Moakley Daniel F, Campbell Melissa, Anglada-Girotto Miquel, Feng Huijuan, Califano Andrea, Au Edmund, Zhang Chaolin
Department of Systems Biology, Columbia University, New York, NY 10032, USA; Department of Biochemistry and Molecular Biophysics, Columbia University, New York, NY 10032, USA; Center for Motor Neuron Biology and Disease, Columbia University, New York, NY 10032, USA.
Department of Systems Biology, Columbia University, New York, NY 10032, USA.
Cell Rep. 2025 Jun 24;44(7):115898. doi: 10.1016/j.celrep.2025.115898.
Cell-type-specific alternative splicing (AS) enables differential gene isoform expression between diverse neuron types with distinct identities and functions. Current studies linking individual RNA-binding proteins (RBPs) to AS in a limited number of neuron types underscore the need for holistic modeling. Here, we use network reverse engineering to derive a map of the neuron-type-specific AS-regulatory landscape of 133 mouse neocortical cell types using pseudobulk transcriptomes derived from single-cell data. We infer the regulons of 350 RBPs and their cell-type-specific activities, among which we validate Elavl2 as a key RBP for medial ganglionic eminence (MGE)-specific splicing in GABAergic interneurons using an in vitro embryonic stem cell (ESC) differentiation system. We also identify a module of exons and candidate regulators specific to long- and short-projection neurons across multiple neuronal classes. This study provides a resource for elucidating splicing-regulatory programs that drive neuronal molecular diversity, including those that do not align with gene-expression-based classifications.
细胞类型特异性可变剪接(AS)使得具有不同身份和功能的多种神经元类型之间能够实现差异基因异构体表达。目前将单个RNA结合蛋白(RBP)与有限数量神经元类型中的AS联系起来的研究强调了整体建模的必要性。在这里,我们使用网络逆向工程,利用从单细胞数据中获得的伪批量转录组,绘制了133种小鼠新皮质细胞类型的神经元类型特异性AS调控图谱。我们推断出350种RBP的调控子及其细胞类型特异性活性,其中我们使用体外胚胎干细胞(ESC)分化系统验证了Elavl2是GABA能中间神经元中内侧神经节隆起(MGE)特异性剪接的关键RBP。我们还鉴定了一个跨多个神经元类别的长投射和短投射神经元特有的外显子和候选调控因子模块。这项研究为阐明驱动神经元分子多样性的剪接调控程序提供了一种资源,包括那些与基于基因表达的分类不一致的程序。