Heath H, Jackson C E, Otterud B, Leppert M F
Department of Internal Medicine, University of Utah School of Medicine, Salt Lake City 84132.
Am J Hum Genet. 1993 Jul;53(1):193-200.
Familial benign hypercalcemia (FBH, or hypocalciuric hypercalcemia) is characterized by inheritance, in an autosomal dominant pattern, of lifelong hypercalcemia without hypercalciuria, which is often mistaken for classical primary hyperparathyroidism. Recently, the FBH trait was linked, in four families, to chromosome 3q. We report genetic linkage analysis in 140 persons from five additional families having FBH (65 affected, 67 unaffected, and 8 unclassifiable). In four families, FBH mapped to chromosome 3q, between D3S1215 and D3S20, maximum multipoint lod score 12.9. By contrast, in the fifth kindred FBH mapped to chromosome 19p13.3, tightly linked to the marker loci D19S20 and D19S266 (two-point lod score at recombination fraction = .001 is 3.44 and 3.70, respectively). Thus, the FBH phenotype results from mutations at two separate loci on chromosomes 3q and 19p.
家族性良性高钙血症(FBH,或低钙尿性高钙血症)的特征是呈常染色体显性模式遗传,终身存在高钙血症但无高钙尿症,这种情况常被误诊为典型的原发性甲状旁腺功能亢进症。最近,在四个家族中,FBH性状与3号染色体长臂相关联。我们对另外五个患有FBH的家族中的140人(65名患者、67名未患病者和8名无法分类者)进行了基因连锁分析。在四个家族中,FBH定位于3号染色体长臂,在D3S1215和D3S20之间,最大多点对数优势分数为12.9。相比之下,在第五个家族中,FBH定位于19号染色体短臂13.3区,与标记位点D19S20和D19S266紧密连锁(重组率为0.001时的两点对数优势分数分别为3.44和3.70)。因此,FBH表型是由3号染色体长臂和19号染色体短臂上两个不同位点的突变引起的。