Bergmann M, Kuchelmeister K, Migheli A, Schiffer D, Gullotta F
Institut für Neuropathologie der Universität, Münster, Germany.
Acta Neuropathol. 1993;86(1):105-8. doi: 10.1007/BF00454908.
A case of motor neuron disease (MND) with pallido-luysio-nigral atrophy (PLNA) is reported. The 45-year-old male patient presented with lower motor neuron symptoms and signs of basal ganglia disturbance. He died after a progressive course of 7 months. Neuropathological examination revealed motor neuron loss at all spinal cord levels with sparing of Onuf's nucleus. Nerve cell loss and gliosis were also present in substantia nigra, globus pallidus, and subthalamic nucleus. The presence of ubiquitin-positive inclusions, a hallmark of most variants of MND, confirms this case as an example of MND. At immunoelectron microscopy the granules were distributed on filamentous material. The combination of clinically apparent PLNA with MND has only been described twice previously. The relationship of this syndrome to other forms of MND and its nosological placement are discussed.
报告了一例患有苍白球-路易体-黑质萎缩(PLNA)的运动神经元病(MND)病例。该45岁男性患者表现出下运动神经元症状和基底节功能障碍的体征。在经历了7个月的进行性病程后死亡。神经病理学检查显示,脊髓各节段均有运动神经元丢失,Onuf核未受累。黑质、苍白球和丘脑底核也存在神经细胞丢失和胶质细胞增生。泛素阳性包涵体的存在是大多数MND变体的一个标志,证实该病例为MND的一个实例。免疫电子显微镜检查显示,颗粒分布于丝状物质上。临床上明显的PLNA与MND的组合此前仅被描述过两次。讨论了该综合征与其他形式MND的关系及其疾病分类归属。