Coon H, Jensen S, Hoff M, Holik J, Plaetke R, Reimherr F, Wender P, Leppert M, Byerley W
Department of Psychiatry, University of Utah Medical Center, Salt Lake City.
Am J Hum Genet. 1993 Jun;52(6):1234-49.
Manic-depressive illness (MDI), also known as "bipolar affective disorder," is a common and devastating neuropsychiatric illness. Although pivotal biochemical alterations underlying the disease are unknown, results of family, twin, and adoption studies consistently implicate genetic transmission in the pathogenesis of MDI. In order to carry out linkage analysis, we ascertained eight moderately sized pedigrees containing multiple cases of the disease. For a four-allele marker mapping 5 cM from the disease gene, the pedigree sample has > 97% power to detect a dominant allele under genetic homogeneity and has > 73% power under 20% heterogeneity. To date, the eight pedigrees have been genotyped with 328 polymorphic DNA loci throughout the genome. When autosomal dominant inheritance was assumed, 273 DNA markers gave lod scores < -2.0 at recombination fraction (theta) = .0, 174 DNA loci produced lod scores < -2.0 at theta = .05, and 4 DNA marker loci yielded lod scores > 1 (chromosome 5--D5S39, D5S43, and D5S62; chromosome 11--D11S85). Of the markers giving lod scores > 1, only D5S62 continued to show evidence for linkage when the affected-pedigree-member method was used. The D5S62 locus maps to distal 5q, a region containing neurotransmitter-receptor genes for dopamine, norepinephrine, glutamate, and gamma-aminobutyric acid. Although additional work in this region may be warranted, our linkage results should be interpreted as preliminary data, as 68 unaffected individuals are not past the age of risk.
躁郁症(MDI),也被称为“双相情感障碍”,是一种常见且具有破坏性的神经精神疾病。尽管该疾病潜在的关键生化改变尚不清楚,但家族、双胞胎和收养研究结果一致表明基因传递在MDI的发病机制中起作用。为了进行连锁分析,我们确定了8个包含多例该疾病的中等规模家系。对于一个距疾病基因5厘摩(cM)定位的四等位基因标记,在基因同质性条件下,家系样本检测显性等位基因的能力大于97%,在20%异质性条件下能力大于73%。迄今为止,已对这8个家系的整个基因组中的328个多态性DNA位点进行了基因分型。假设为常染色体显性遗传时,在重组率(θ)=0时,273个DNA标记的对数优势比(lod)得分<-2.0;在θ=0.05时,174个DNA位点的lod得分<-2.0;4个DNA标记位点的lod得分>1(5号染色体——D5S39、D5S43和D5S62;11号染色体——D11S85)。在lod得分>1的标记中,当使用患病家系成员法时,只有D5S62继续显示出连锁证据。D5S62位点定位于5q远端,该区域包含多巴胺、去甲肾上腺素、谷氨酸和γ-氨基丁酸的神经递质受体基因。尽管该区域可能需要进一步研究,但我们的连锁结果应被视为初步数据,因为68名未患病个体尚未超过发病风险年龄。