Mahtani M M, Widén E, Lehto M, Thomas J, McCarthy M, Brayer J, Bryant B, Chan G, Daly M, Forsblom C, Kanninen T, Kirby A, Kruglyak L, Munnelly K, Parkkonen M, Reeve-Daly M P, Weaver A, Brettin T, Duyk G, Lander E S, Groop L C
Whitehead Institute for Biomedical Research, Cambridge, Massachusetts 02142, USA.
Nat Genet. 1996 Sep;14(1):90-4. doi: 10.1038/ng0996-90.
Non-insulin dependent diabetes mellitus (NIDDM) affects more than 100 million people worldwide and is associated with severe metabolic defects, including peripheral insulin resistance, elevated hepatic glucose production, and inappropriate insulin secretion. Family studies point to a major genetic component, but specific susceptibility genes have not yet been identified-except for rare early-onset forms with monogenic or mitochondrial inheritance. We have screened over 4,000 individuals from a population isolate in western Finland, identified 26 families (comprising 217 individuals) enriched for NIDDM and performed a genome-wide scan using non-parametric linkage analysis. We found no significant evidence for linkage when the families were analysed together, but strong evidence for linkage when families were classified according to mean insulin levels in affecteds (in oral glucose tolerance tests). Specifically, families with the lowest insulin levels showed linkage (P = 2 x 10(-6)) to chromosome 12 near D12S1349. Interestingly, this region contains the gene causing the rare, dominant, early-onset form of diabetes MODY3. Unlike MODY3 families, the Finnish families with low insulin have an age-of-onset typical for NIDDM (mean = 58 years). We infer the existence of a gene NIDDM2 causing NIDDM associated with low insulin secretion, and suggest that NIDDM2 and MODY3 may represent different alleles of the same gene.
非胰岛素依赖型糖尿病(NIDDM)在全球影响着超过1亿人,与严重的代谢缺陷相关,包括外周胰岛素抵抗、肝脏葡萄糖生成增加以及胰岛素分泌异常。家族研究表明存在主要的遗传成分,但除了罕见的具有单基因或线粒体遗传的早发型形式外,尚未确定具体的易感基因。我们对来自芬兰西部一个人群隔离区的4000多人进行了筛查,确定了26个富含NIDDM的家族(共217人),并使用非参数连锁分析进行了全基因组扫描。当一起分析这些家族时,我们没有发现连锁的显著证据,但当根据受影响者(口服葡萄糖耐量试验)的平均胰岛素水平对家族进行分类时,发现了连锁的有力证据。具体而言,胰岛素水平最低的家族显示与12号染色体上靠近D12S1349的区域连锁(P = 2×10⁻⁶)。有趣的是,该区域包含导致罕见的显性早发型糖尿病MODY3的基因。与MODY3家族不同,胰岛素水平低的芬兰家族具有NIDDM典型的发病年龄(平均 = 58岁)。我们推断存在一个导致与低胰岛素分泌相关的NIDDM的基因NIDDM2,并表明NIDDM2和MODY3可能代表同一基因的不同等位基因。