Bloom A L
Schweiz Med Wochenschr. 1979 Sep 29;109(37):1357-61.
Factor VIII is a complex molecule comprising a series of homologous oligomers with biological activity related to primary haemostasis (factor VIII related antigen/Willebrand factor; FVIIIRAg/WF). The structure or distribution of these oligomers is abnormal in von Willebrand's disease (vWd). The oligomers are associated with, or contain, a lower molecular weight entity with procoagulant activity (factor VIIIC) which has distinct antigenic determinants and is reduced or abnormal in haemophilia. Recessive and dominant forms of vWd have been recognised but two families are described each with features of both dominant and recessive inheritance; this is of importance in genetic counselling. Results of a new immunoradiometric assay for factor VIIIC antigen showed reduced levels in vWd and haemophilia and it was absent in 3 of 6 samples from fetuses of obligate carriers of haemophilia. The potential use of this assay for the prenatal diagnosis of haemophilia is described.
凝血因子VIII是一种复杂分子,由一系列同源寡聚体组成,其生物活性与初级止血相关(因子VIII相关抗原/血管性血友病因子;FVIIIRAg/WF)。在血管性血友病(vWd)中,这些寡聚体的结构或分布异常。这些寡聚体与具有促凝血活性的较低分子量实体(因子VIIIC)相关联或包含该实体,因子VIIIC具有独特的抗原决定簇,在血友病中含量减少或异常。已识别出vWd的隐性和显性形式,但描述了两个家族,每个家族都具有显性和隐性遗传的特征;这在遗传咨询中很重要。一种针对因子VIIIC抗原的新型免疫放射分析方法的结果显示,vWd和血友病患者中该抗原水平降低,在血友病携带者胎儿的6份样本中有3份未检测到该抗原。本文描述了该检测方法在血友病产前诊断中的潜在应用。