Léauté-Labrèze C, Depaire-Duclos F, Sarlangue J, Fontan D, Sandler B, Maleville J, Taïeb A
Pediatric Dermatology Unit, Hôpital Pellegrin-Enfants, Bordeaux, France.
Arch Dermatol. 1998 Sep;134(9):1121-4. doi: 10.1001/archderm.134.9.1121.
During twin pregnancies, several complications may result in the death of a co-twin depending on the date of death. We describe herein 2 infant survivors of monozygotic twin pairs with 2 distinct possible complications: a aplasia cutis congenita and Volkmann ischemic contracture.
One infant had extensive aplasia cutis congenita with an associated monozygotic co-twin who died at 3 months of gestation, and the other child had a localized arm defect due to Volkmann ischemic contracture and brain damage, with a co-twin who died at approximately 6 weeks of gestation.
Congenital cutaneous defects may result in the death of a co-twin. The most common of these defects is aplasia cutis congenita associated with a fetus papyraceus or a dead fetus related to ischemic/thrombotic events in the placenta and fetus. Volkmann ischemic contracture is rare in the newborn but can cause neonatal cutaneous defects. The cause of Volkmann ischemic contracture in newborns is unknown; however, our second observation suggests the possible role of a dead fetus.
在双胎妊娠期间,根据死亡时间的不同,多种并发症可能导致其中一个胎儿死亡。我们在此描述了2例单卵双胎的婴儿幸存者,他们出现了2种不同的可能并发症:先天性皮肤发育不全和福克曼缺血性挛缩。
一名婴儿患有广泛的先天性皮肤发育不全,其单卵双胎在妊娠3个月时死亡;另一名儿童因福克曼缺血性挛缩和脑损伤出现局部手臂缺陷,其双胎在妊娠约6周时死亡。
先天性皮肤缺陷可能导致双胎中的一个胎儿死亡。这些缺陷中最常见的是与纸样胎儿或与胎盘和胎儿缺血/血栓形成事件相关的死胎相关的先天性皮肤发育不全。福克曼缺血性挛缩在新生儿中罕见,但可导致新生儿皮肤缺陷。新生儿福克曼缺血性挛缩的病因尚不清楚;然而,我们的第二个观察结果提示了死胎可能起到的作用。