Sharma J, Sehgal K V, Harmon R L
Department of Physical Medicine and Rehabilitation, Medical College of Ohio, Toledo 43614-5807, USA.
Am J Phys Med Rehabil. 1998 Sep-Oct;77(5):455-7. doi: 10.1097/00002060-199809000-00021.
Moyamoya disease is a rare disorder of cerebrovascular circulation. A review of the literature failed to reveal the association of heterotopic ossification in patients with this disease; such a case is now presented. The patient described had atraumatic intracranial hemorrhage, was in a coma for a period of time, underwent ventriculostomy and shunt placement, and was left with residual spastic hemiparesis. Evidence of heterotopic ossification around the hemiparetic shoulder and hip was subsequently noted on radiographic studies and was managed conservatively. Heterotopic ossification may be a rare complication of the neurological deficits associated with moyamoya disease and needs careful consideration when joint stiffness persists, despite usual conservative measures.
烟雾病是一种罕见的脑血管循环障碍疾病。对文献的回顾未能揭示该疾病患者发生异位骨化的关联；现报告这样一例病例。所述患者发生非创伤性颅内出血，昏迷一段时间，接受了脑室造瘘术和分流管置入术，遗留残余痉挛性偏瘫。随后影像学检查发现偏瘫侧肩部和髋部周围存在异位骨化证据，并采取了保守治疗。异位骨化可能是烟雾病相关神经功能缺损的一种罕见并发症，当尽管采取了常规保守措施但关节僵硬仍持续存在时，需要仔细考虑。
