Weber P, Bartsch U, Schachner M, Montag D
Department of Neurobiology, Swiss Federal Institute of Technology, CH-8093 Zürich, Switzerland.
J Neurosci. 1998 Nov 15;18(22):9192-203. doi: 10.1523/JNEUROSCI.18-22-09192.1998.
The beta2 subunit of the Na,K-ATPase displays functional properties of both an integral constituent of an ion pump and an adhesion and neurite outgrowth-promoting molecule in vitro. To investigate whether the beta1 subunit of the Na,K-ATPase can functionally substitute for the beta2 isoform in vivo, we have generated beta2/beta1 knock-in mice by homologous recombination in embryonic stem cells. In beta2/beta1 knock-in mice, expression of beta2 was abolished, whereas beta1 mRNA expression from the mutated gene amounted to approximately 15% of the normal expression of beta2 in the adult mouse brain and prevented the juvenile lethality observed for beta2 null mutant mice. In contrast to beta2 null mutant mice, the overall morphological structure of all analyzed brain regions was normal. By immunohistochemical analysis, beta1 expression was detected in photoreceptor cells in the retina of knock-in mice at an age when expression of beta1 and beta2, respectively, is downregulated and persisting in the wild-type mice. Morphological analysis by light and electron microscopy revealed a progressive degeneration of photoreceptor cells. Apoptotic death of photoreceptor cells determined quantitatively by terminal deoxynucleotidyl transferase-mediated dUTP nick end labeling analysis increased in beta2/beta1 knock-in mice with age. These observations suggest that the beta1 subunit of the Na,K-ATPase can substitute sufficiently, at least in certain cell types, for the role of the beta2 subunit as a component of a functional Na,K-ATPase, but they do not allow us to determine the possible role of the beta2 subunit as an adhesion molecule in vivo.
钠钾ATP酶的β2亚基在体外既表现出离子泵不可或缺的组成部分的功能特性,又具有促进黏附及神经突生长的分子的功能特性。为了研究钠钾ATP酶的β1亚基在体内是否能在功能上替代β2亚型,我们通过胚胎干细胞中的同源重组产生了β2/β1基因敲入小鼠。在β2/β1基因敲入小鼠中,β2的表达被消除,而突变基因的β1 mRNA表达量约为成年小鼠大脑中β2正常表达量的15%,并防止了β2基因敲除突变小鼠出现的幼年致死现象。与β2基因敲除突变小鼠不同,所有分析脑区的整体形态结构均正常。通过免疫组织化学分析,在基因敲入小鼠视网膜的光感受器细胞中检测到β1表达,而在这个年龄段,野生型小鼠中β1和β2的表达分别下调并持续存在。光镜和电镜形态学分析显示光感受器细胞进行性退化。通过末端脱氧核苷酸转移酶介导的dUTP缺口末端标记分析定量测定的光感受器细胞凋亡死亡在β2/β1基因敲入小鼠中随年龄增加。这些观察结果表明,钠钾ATP酶的β1亚基至少在某些细胞类型中可以充分替代β2亚基作为功能性钠钾ATP酶组成部分的作用,但它们无法让我们确定β2亚基在体内作为黏附分子的可能作用。