Demura R, Demura H, Shizume K, Kubo O, Kitamura K
Endocrinol Jpn. 1976 Jun;23(3):215-9. doi: 10.1507/endocrj1954.23.215.
A female case of precocious puberty associated with HCG-producing ectopic pinealoma was reported. The patient, a 5-year-old girl, was referred to the hospital because of headache and choked discs. Physical examination revealed normal physical growth with breast enlargement. Endocrinological study revealed a high plasma HCG concentration of 1192 ng/ml with a normal FSH level. None of HCG, LH and FSH did respond to the LH-RH test. A partial resection of the tumor and an external X-ray irradiation relieved the symptoms and breast enlargement subsided with a remarkable decrease in the plasma HCG level. Histological examination revealed two-cell-pattern pinealoma and electron microscopic findings showed abundant secretory granules in the dark cells. HCG content in the tumor was as high was 400 ng/mg of acetone dried tumor tissue, but no FSH was detectable. Hitherto, all of the reported cases of precocious puberty associated with pineal tumors have been exclusively boys. A normal level of plasma FSH concentration with a somewhat elevated prolactin level might be a contributory factor for the development of precocial sexual development in the present case.
报告了一例与产生人绒毛膜促性腺激素(HCG)的异位松果体瘤相关的性早熟女性病例。该患者为一名5岁女孩,因头痛和视乳头水肿被转诊至医院。体格检查显示身体生长正常,但乳房增大。内分泌学研究显示血浆HCG浓度高达1192 ng/ml,卵泡刺激素(FSH)水平正常。HCG、促黄体生成素(LH)和FSH对促性腺激素释放激素(LH-RH)试验均无反应。肿瘤部分切除及体外X线照射缓解了症状,乳房增大消退,血浆HCG水平显著下降。组织学检查显示为两细胞型松果体瘤,电子显微镜检查发现暗细胞中有丰富的分泌颗粒。肿瘤中的HCG含量高达400 ng/mg丙酮干燥肿瘤组织,但未检测到FSH。迄今为止,所有报道的与松果体肿瘤相关的性早熟病例均为男性。血浆FSH浓度正常而催乳素水平略有升高可能是本例性早熟发展的一个促成因素。