Matiz S, Tamariz-Martel R, Cazzaniga M, Vázquez Martínez J, Villagrá Blanco F
Servicio de Cardiología Pediátrica, Hospital Ramón y Cajal, Madrid.
An Esp Pediatr. 2001 Apr;54(4):397-401.
We present a newborn infant with right atrial isomerism, complex congenital heart malformation and anomalous pulmonary venous connection, reliably diagnosed by 2-D Doppler color echocardiography. The infant had no significant obstetric antecedents. The neonatal clinical picture included cyanosis, heart murmur and respiratory distress. The infant was treated with prostaglandin from the age of 24 hours until his death after surgery. The 2-D echo Doppler color flow mapping showed findings that suggested right atrial isomerism, severe left ventricular hypoplasia, pulmonary atresia and ductus arteriosus. The pulmonary veins flowed together to a posterior cardiac chamber from which an emissary vertical venous vessel connected with a left superior aneurysmal sack. Two venous channels emerged from this sack: one connecting to the innominate vein and the other to the atrium. The malformations were confirmed by cardiac catheterization. On the sixth day of life, the patient underwent anastomosis between the posterior venous chamber with the atrium, a modified Blalock-Taussig shunt implant, and ductus closure but died during surgery. The association between complex cardiac anomalies and uncommon obstructive total anomalous pulmonary venous connection in the context of right atrial isomerism is lethal and few neonates survive surgical repair. Two-dimensional echo color flow Doppler is a reliable diagnostic technique and an indispensable guide in angiography.
我们报告一名患有右心房异构、复杂先天性心脏畸形及异常肺静脉连接的新生儿,通过二维多普勒彩色超声心动图得以可靠诊断。该婴儿无明显产科病史。新生儿临床表现包括发绀、心脏杂音及呼吸窘迫。该婴儿自出生24小时起接受前列腺素治疗,直至术后死亡。二维超声多普勒彩色血流图显示提示右心房异构、严重左心室发育不全、肺动脉闭锁及动脉导管未闭的表现。肺静脉共同汇入一个后心腔,一条垂直的静脉分支从该心腔与左上动脉瘤样囊相连。从该囊中发出两条静脉通道:一条连接到无名静脉,另一条连接到心房。心脏导管检查证实了这些畸形。在出生后第六天,患者接受了后静脉腔与心房之间的吻合术、改良布莱洛克 - 陶西格分流术植入及动脉导管闭合术,但在手术过程中死亡。在右心房异构的情况下,复杂心脏异常与罕见的梗阻性完全性肺静脉异常连接之间的关联是致命的,很少有新生儿能在手术修复后存活。二维超声彩色血流多普勒是一种可靠的诊断技术,也是血管造影中不可或缺的指导手段。