Harada Katsuhisa, Noguchi Tsuyoshi, Miura Takashi, Kawano Youzo, Kashima Kenji, Kawahara Katsunobu
Department of Oncological Science (Surgery II), Oita University Faculty of Medicine, Yufu, Japan.
Jpn J Thorac Cardiovasc Surg. 2005 Oct;53(10):580-2. doi: 10.1007/s11748-005-0073-z.
We report a case of a 29 year old male who at age 25, developed a pulmonary abscess in the left lower lobe. A left lower lobectomy was performed following two recurrences on antibiotic treatment. The result of histopathological examination confirmed congenital cystic adenomatoid malformation (CCAM), a congenital disease characterized by multiple cysts resulting from adenomatous hyperplasia of the bronchial epithelia. In many cases, respiratory distress occurs during the neonatal period, and in about 80-85% of patients, CCAM is diagnosed before the age of two years due to respiratory infection. CCAM which was diagnosed in adulthood is very rare.
我们报告一例29岁男性病例,该患者25岁时左下叶出现肺脓肿。在抗生素治疗后两次复发,随后进行了左下叶切除术。组织病理学检查结果证实为先天性囊性腺瘤样畸形(CCAM),这是一种先天性疾病,其特征是支气管上皮腺瘤样增生导致多个囊肿。在许多病例中,新生儿期会出现呼吸窘迫,约80-85%的患者因呼吸道感染在两岁前被诊断出CCAM。成年期诊断出的CCAM非常罕见。