Oak Jean S, Deane Jonathan A, Kharas Michael G, Luo Ji, Lane Thomas E, Cantley Lewis C, Fruman David A
Department of Molecular Biology and Biochemistry, University of California, Irvine, CA 92697-3900, USA.
Proc Natl Acad Sci U S A. 2006 Nov 7;103(45):16882-7. doi: 10.1073/pnas.0607984103. Epub 2006 Oct 27.
Sjögren's syndrome (SS) is an autoimmune disease that is characterized by infiltration of exocrine tissues, resulting in xerostomia (dry mouth) and keratoconjunctivitis sicca (dry eyes). Here, we show that mice with T cell-specific loss of class IA phosphoinositide 3-kinase function develop organ-specific autoimmunity that resembles the human disease SS. Most mutant mice aged 3-8 months develop corneal opacity and eye lesions due to irritation and constant scratching. These mice display cardinal signs of primary SS such as marked lymphocytic infiltration of the lacrimal glands, antinuclear antibodies in the serum, and elevated titer of anti-SS-A antibody, in the absence of kidney pathology. Immunofluorescence studies show the presence of numerous CD4+ T cells with a smaller number of CD8+ T cells and B cells in the lacrimal glands. CD4+ T cells from these mice exhibit aberrant differentiation in vitro. These results indicate that aberrant T cells with impaired class IA phosphoinositide 3-kinase signaling can lead to organ-specific autoimmunity. In addition, the mouse model described here represents a tool to study the pathogenesis and treatment of SS.
干燥综合征(SS)是一种自身免疫性疾病,其特征是外分泌组织浸润,导致口干症(口干)和干燥性角结膜炎(干眼)。在此,我们表明,IA类磷酸肌醇3激酶功能在T细胞特异性缺失的小鼠会发生类似于人类疾病SS的器官特异性自身免疫。大多数3至8个月大的突变小鼠由于刺激和持续抓挠而出现角膜混浊和眼部病变。这些小鼠表现出原发性SS的主要体征,如泪腺明显的淋巴细胞浸润、血清中的抗核抗体以及抗SS-A抗体滴度升高,且无肾脏病变。免疫荧光研究显示泪腺中有大量CD4+ T细胞,以及数量较少的CD8+ T细胞和B细胞。来自这些小鼠的CD4+ T细胞在体外表现出异常分化。这些结果表明,IA类磷酸肌醇3激酶信号传导受损的异常T细胞可导致器官特异性自身免疫。此外,这里描述的小鼠模型是研究SS发病机制和治疗的一种工具。