Chitayat D, Meunier C M, Hodgkinson K A, Silver K, Flanders M, Anderson I J, Little J M, Whiteman D A, Carpenter S
Department of Pediatrics, Montreal Childrens Hospital, Quebec, Canada.
Am J Med Genet. 1991 Dec 1;41(3):313-8. doi: 10.1002/ajmg.1320410310.
The clinical manifestations and psychomotor development of five patients with mucolipidosis IV (MLIV) from three Ashkenazi-Jewish families are reported. The presenting symptoms were hypotonia, developmental delay, corneal clouding, and puffy eyelids. Four of the patients had convergent strabismus and none progressed beyond a developmental age of 15 months. One patient died of aspiration at 17 years while the oldest patient entered puberty at 20 years, developed a coarse face at 30 years, and is now 32 years old. Histopathological studies in four patients showed storage changes characteristic of MLIV.
报告了来自三个阿什肯纳兹犹太家庭的五名黏脂贮积症IV型(MLIV)患者的临床表现和精神运动发育情况。主要症状为肌张力减退、发育迟缓、角膜混浊和眼睑肿胀。其中四名患者有内斜视,且发育年龄均未超过15个月。一名患者17岁时死于误吸,而年龄最大的患者20岁进入青春期,30岁时面部变得粗糙,现32岁。对四名患者的组织病理学研究显示出MLIV特有的贮积变化。