Rouster-Stevens Kelly A, Pachman Lauren M
Wake Forest University School of Medicine, Department of Pediatrics/Pediatric Rheumatology, Winston-Salem, North Carolina 27157, USA.
J Rheumatol. 2008 May;35(5):927-9. Epub 2008 Mar 1.
Anti-signal recognition particle (anti-SRP) is a myositis-specific autoantibody that is linked to a severe polymyositis (PM) associated with interstitial lung disease (ILD) and esophageal dysmotility in adults. We describe 3 African American adolescent girls with anti-SRP juvenile PM. One child required aggressive treatment to control her disease and 2 were refractory to multiple immunosuppressants. Patient 1 developed ILD and cardiac disease; Patient 2 developed ILD; Patient 3 developed esophageal dysmotility and cardiac disease. Organ system involvement was comparable to that seen in adults. We conclude that testing for anti-SRP in children with PM may facilitate diagnosis and management.
抗信号识别颗粒(anti-SRP)是一种肌炎特异性自身抗体,与成人严重的多发性肌炎(PM)相关,后者伴有间质性肺疾病(ILD)和食管动力障碍。我们描述了3例患有抗SRP青少年型PM的非裔美国少女。1名儿童需要积极治疗以控制病情,另外2名对多种免疫抑制剂均无效。患者1出现了ILD和心脏疾病;患者2出现了ILD;患者3出现了食管动力障碍和心脏疾病。器官系统受累情况与成人所见相当。我们得出结论,对患有PM的儿童进行抗SRP检测可能有助于诊断和治疗。