Pribila Jonathan T, Ronan Shawn M, Trobe Jonathan D
Department of Ophthalmology, Kellogg Eye Center, University of Michigan, Ann Arbor, Michigan, USA.
J Neuroophthalmol. 2008 Mar;28(1):41-6. doi: 10.1097/WNO.0b013e318167540e.
A 27-year-old man with nevoid basal cell carcinoma syndrome (NBCCS, Gorlin syndrome) who had undergone craniospinal irradiation for a childhood brain stem medulloblastoma complained of progressive binocular visual loss. Ophthalmologic examination disclosed subnormal visual acuity and visual fields in both eyes attributed to chronic papilledema. Brain MRI demonstrated mass effect from multiple large meningiomas. After embolization and surgical resection of the largest meningioma, papilledema disappeared and visual dysfunction resolved partially. This is the sixth reported patient with NBCCS, medulloblastoma, and craniospinal radiation who has developed intracranial meningioma, further documenting the fact that such patients have a relatively high likelihood of developing meningiomas, especially multiple meningiomas. Because patients with NBCCS are often mentally impaired and because papilledema can progress silently before causing irreversible visual loss, periodic ophthalmologic examination is advisable after craniospinal radiation.
一名患有痣样基底细胞癌综合征(NBCCS,戈林综合征)的27岁男性,童年时因脑干髓母细胞瘤接受了颅脊髓照射,现主诉双眼视力进行性丧失。眼科检查发现双眼视力和视野低于正常,归因于慢性视乳头水肿。脑部MRI显示多个大型脑膜瘤产生的占位效应。对最大的脑膜瘤进行栓塞和手术切除后,视乳头水肿消失,视觉功能障碍部分缓解。这是第六例报告的患有NBCCS、髓母细胞瘤和接受颅脊髓放疗后发生颅内脑膜瘤的患者,进一步证明了此类患者发生脑膜瘤尤其是多发性脑膜瘤的可能性相对较高。由于NBCCS患者常伴有智力障碍,且视乳头水肿在导致不可逆视力丧失之前可能会悄然进展,因此在颅脊髓放疗后建议定期进行眼科检查。