Travis Jennifer, Varma Anoop, duPlessis Daniel, Turnbull Ian, Vilar F Javier
Monsall Unit, Department of Infectious Diseases and Tropical Medicine, North Manchester General Hospital, Crumpsall, Manchester, UK.
Neurologist. 2008 Sep;14(5):321-6. doi: 10.1097/NRL.0b013e31816e2f13.
To report the neuropathological findings of a patient with immune reconstitution syndrome associated with progressive multifocal leukoencephalopathy (PML) in human immunodeficiency virus (HIV) and to review the literature.
A 38-year-old man was presented with a rapidly evolving brainstem syndrome. Serology for HIV was positive with an initial CD4 count of 130 cells/mL3. Magnetic resonance imaging showed widespread high signal changes within the brainstem bilaterally, the cerebellum, inferior cerebellar peduncle, and the frontal lobe on the right. Opportunistic infections were excluded from blood and cerebrospinal fluid samples. Despite treatment with antiretrovirals, he continued to deteriorate neurologically, and a repeat magnetic resonance imaging scan showed progression of his lesions. Cortical wedge frontal lobe brain biopsy showed features characteristic of PML, but was associated with an exaggerated inflammatory response. Polymerase chain reaction analysis of the specimen demonstrated the presence of JC virus (JCV) DNA, confirming the pathologic impression of PML.
The patient made a rapid (within 24 hours) improvement with pulsed methylprednisolone and has maintained a clinical response 7 months later. These features clinically, radiologically, and histopathologically suggest an added component in the form of immune reconstitution syndrome to PML.
This report highlights the need to carefully evaluate the clinical syndrome in patients with HIV-associated leukoencephalopathy. It also substantiates the role of corticosteroids in carefully considered cases of HIV with leukoencephalopathy secondary to immune reconstitution.
报告1例与进行性多灶性白质脑病(PML)相关的免疫重建综合征患者的神经病理学发现,并复习相关文献。
1例38岁男性患者,表现为快速进展的脑干综合征。HIV血清学检测呈阳性,初始CD4细胞计数为130个/ mL³。磁共振成像显示双侧脑干、小脑、小脑下脚及右侧额叶广泛高信号改变。血液和脑脊液样本排除了机会性感染。尽管接受了抗逆转录病毒治疗,但患者神经功能仍持续恶化,重复磁共振成像扫描显示病变进展。额叶皮质楔形脑活检显示PML特征性表现,但伴有过度炎症反应。标本的聚合酶链反应分析显示存在JC病毒(JCV)DNA,证实了PML的病理诊断。
患者接受脉冲甲基强的松龙治疗后迅速(24小时内)改善,7个月后仍保持临床缓解。这些临床、影像学和组织病理学特征提示PML中存在免疫重建综合征这一附加成分。
本报告强调了仔细评估HIV相关白质脑病患者临床综合征的必要性。它也证实了皮质类固醇在经过仔细考虑的HIV继发免疫重建白质脑病病例中的作用。