Unit of Rheumatology, Interdepartmental Research Center of Systemic Autoimmune and Autoinflammatory Diseases, Policlinico Le Scotte, University of Siena, Viale Bracci 1, 53100 Siena, Italy.
Rheumatol Int. 2012 Feb;32(2):465-7. doi: 10.1007/s00296-009-1331-7. Epub 2010 Jan 1.
Systemic juvenile idiopathic arthritis (SJIA) is a disorder characterized by arthritis in children starting before 16 years of age associated with daily high fever, persisting for more than 2 weeks, and at least one of the following clinical features: evanescent cutaneous rash, lymphadenopathy, serositis or hepatosplenomegaly. SJIA patients carry a significantly higher frequency of MEFV mutations, the gene responsible for familial Mediterranean fever, and may be characterized by a more aggressive disease. In this line, we describe a 9-year-old girl affected with SJIA who carried a heterozygous G196W mutation in MEFV. Our patient was characterized by an aggressive disease course, resistance to conventional immunosuppressive agents and developed renal amyloidosis just 2 years after the disease onset.
全身型幼年特发性关节炎(SJIA)是一种以 16 岁以下儿童关节炎为特征的疾病,与每日高热相关,持续超过 2 周,且至少有以下一种临床特征:一过性皮疹、淋巴结病、浆膜炎或肝脾肿大。SJIA 患者 MEFV 基因突变频率明显更高,MEFV 基因是家族性地中海热的致病基因,疾病可能更具侵袭性。在此方面,我们描述了一名患有 SJIA 的 9 岁女孩,她携带 MEFV 的杂合 G196W 突变。我们的患者疾病进展迅速,对常规免疫抑制剂耐药,并在发病后 2 年内就发展为肾淀粉样变性。