Koopmans P P, Bodeutsch C, de Wilde P C, Boerbooms A M
Department of Medicine, University Hospital, Nijmegen, The Netherlands.
Ann Rheum Dis. 1990 Jun;49(6):407-9. doi: 10.1136/ard.49.6.407.
A 45 year old man, previously diagnosed as having sarcoid, presented with signs and symptoms of a pancreatic malignancy. An explorative laparotomy, however, showed only chronic pancreatitis. He was found to have a raised erythrocyte sedimentation rate, normocytic normochromic anaemia, renal insufficiency, hypergammaglobulinaemia, and a strongly positive rheumatoid factor and antinuclear antibody titre. Bilateral hilar lymph node enlargement was noted on chest x ray. Subsequently, the patient complained of xerostomia and keratoconjunctivitis sicca. Large lymphocytic infiltrates and a shift in the relative number of IgA bearing plasma cells in favour of IgG and IgM bearing plasma cells were seen in tissue obtained by sublabial salivary gland biopsy. A transbronchial lung biopsy and review of the biopsies of the pancreas, the lung, liver, and a lymph node all failed to show granulomatous disease. These findings strongly suggested a diagnosis of Sjögren's syndrome instead of sarcoidosis. This case shows the difficulty sometimes encountered in differentiating between sarcoid and systemic Sjögren's syndrome, and the value of a sublabial salivary gland biopsy.
一名45岁男性,既往诊断为结节病,现出现胰腺恶性肿瘤的体征和症状。然而,剖腹探查仅显示为慢性胰腺炎。发现他红细胞沉降率升高、正细胞正色素性贫血、肾功能不全、高球蛋白血症、类风湿因子和抗核抗体滴度强阳性。胸部X线检查发现双侧肺门淋巴结肿大。随后,患者出现口干和干燥性角结膜炎。唇下唾液腺活检组织可见大量淋巴细胞浸润,且携带IgA的浆细胞相对数量减少,有利于携带IgG和IgM的浆细胞。经支气管肺活检以及对胰腺、肺、肝脏和淋巴结活检的复查均未发现肉芽肿性疾病。这些发现强烈提示诊断为干燥综合征而非结节病。该病例显示了结节病与系统性干燥综合征鉴别有时存在的困难,以及唇下唾液腺活检的价值。