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一名类风湿关节炎患者反复出现自发性皮下气肿。

Recurrent spontaneous subcutaneous emphysema in a patient with rheumatoid arthritis.

作者信息

Adelowo Olufemi, Akintayo Richard Oluyinka, Olaosebikan Hakeem, Oba Rasheedat

机构信息

Rheumatology Unit, Department of Medicine, Lagos State University Teaching Hospital, Ikeja, Lagos, Nigeria.

Department of Medicine, University of Ilorin Teaching Hospital, Ilorin, Nigeria.

出版信息

BMJ Case Rep. 2015 Oct 15;2015:bcr2015210802. doi: 10.1136/bcr-2015-210802.

Abstract

Pulmonary air leak syndromes are extremely rare complications of systemic autoimmune connective tissue diseases and the occurrence of spontaneous subcutaneous emphysema (SSE) from pulmonary leak in the absence of pneumothorax or pneumomediastinum is even rarer. We report a case of recurrent SSE in a patient with rheumatoid arthritis and interstitial lung disease. The SSE was managed conservatively each time and it resorbed over several days. There has been no previous documented report of SSE in the absence of pneumomediastinum, pneumothorax or pulmonary nodules in a patient with RA.

摘要

肺空气泄漏综合征是系统性自身免疫性结缔组织病极为罕见的并发症,在无气胸或纵隔气肿的情况下因肺漏气发生自发性皮下气肿(SSE)则更为罕见。我们报告1例类风湿关节炎合并间质性肺疾病患者反复发生SSE的病例。每次SSE均采用保守治疗,数天内自行吸收。此前尚无关于类风湿关节炎患者在无纵隔气肿、气胸或肺结节情况下发生SSE的文献报道。

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本文引用的文献

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Recurrent pneumomediastinum in a patient with rheumatoid arthritis.
Monaldi Arch Chest Dis. 2013 Sep-Dec;79(3-4):136-9. doi: 10.4081/monaldi.2013.5213.
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