Univ. Lille, U995, Lille Inflammation Research International Center (LIRIC), Lille, France.
Inserm, U995, Lille, France.
PLoS One. 2018 May 15;13(5):e0197112. doi: 10.1371/journal.pone.0197112. eCollection 2018.
Pre-capillary pulmonary hypertension (PH) in systemic sclerosis (SSc) is a heterogeneous condition with an overall bad prognosis. The objective of this study was to identify and characterize homogeneous phenotypes by a cluster analysis in SSc patients with PH. Patients were identified from two prospective cohorts from the US and France. Clinical, pulmonary function, high-resolution chest tomography, hemodynamic and survival data were extracted. We performed cluster analysis using the k-means method and compared survival between clusters using Cox regression analysis. Cluster analysis of 200 patients identified four homogenous phenotypes. Cluster C1 included patients with mild to moderate risk pulmonary arterial hypertension (PAH) with limited or no interstitial lung disease (ILD) and low DLCO with a 3-year survival of 81.5% (95% CI: 71.4-88.2). C2 had pre-capillary PH due to extensive ILD and worse 3-year survival compared to C1 (adjusted hazard ratio [HR] 3.14; 95% CI 1.66-5.94; p = 0.0004). C3 had severe PAH and a trend towards worse survival (HR 2.53; 95% CI 0.99-6.49; p = 0.052). Cluster C4 and C1 were similar with no difference in survival (HR 0.65; 95% CI 0.19-2.27, p = 0.507) but with a higher DLCO in C4. PH in SSc can be characterized into distinct clusters that differ in prognosis.
特发性肺动脉高压(PH)在系统性硬化症(SSc)中是一种异质性疾病,总体预后较差。本研究的目的是通过聚类分析确定和描述 SSc 合并 PH 患者的同质表型。患者是从美国和法国的两个前瞻性队列中确定的。提取了临床、肺功能、高分辨率胸部 CT、血流动力学和生存数据。我们使用 k-均值法进行聚类分析,并使用 Cox 回归分析比较了各聚类之间的生存情况。对 200 例患者进行聚类分析,确定了 4 种同质表型。聚类 C1 包括中至重度肺动脉高压(PAH)、局限性或无间质性肺病(ILD)和低弥散量(DLCO)的患者,其 3 年生存率为 81.5%(95%CI:71.4-88.2)。C2 存在因广泛 ILD 导致的毛细血管前 PH,与 C1 相比 3 年生存率较差(调整后的危险比[HR]3.14;95%CI 1.66-5.94;p=0.0004)。C3 患者存在严重的 PAH,且生存情况呈下降趋势(HR 2.53;95%CI 0.99-6.49;p=0.052)。C4 和 C1 相似,生存率无差异(HR 0.65;95%CI 0.19-2.27,p=0.507),但 C4 的 DLCO 更高。SSc 中的 PH 可分为不同预后的不同聚类。