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一例罕见的因蝶窦炎并发的化脓性海绵窦血栓形成病例。

A rare case of septic cavernous sinus thrombosis as a complication of sphenoid sinusitis.

作者信息

Chen Ming-Chun, Ho Yu-Huai, Chong Pau-Nyen, Chen Jui-Hsia

机构信息

Department of Pediatrics, Hualien Tzu Chi Hospital, Buddhist Tzu Chi Medical Foundation, Hualien, Taiwan.

Department of Infectious Disease, Hualien Tzu Chi Hospital, Buddhist Tzu Chi Medical Foundation, Hualien, Taiwan.

出版信息

Tzu Chi Med J. 2019 Jan-Mar;31(1):63-65. doi: 10.4103/tcmj.tcmj_1_18.

DOI:10.4103/tcmj.tcmj_1_18
PMID:30692835
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC6334571/
Abstract

Isolated sphenoid sinusitis is a rare disorder and may present with severe complications due to its proximity to the orbital and intracranial areas. We report a 13-year-old boy hospitalized for septic shock with fever of unknown origin. Facial palsy was later noted. Brain magnetic resonance imaging showed a sphenoid mass and right cavernous sinus and internal jugular vein thrombosis. Biopsy revealed chronic rhinosinusitis. Complete recovery followed by an incision/drainage procedure and antibiotic treatment. Acute sphenoid sinusitis should be included in the differential diagnosis of septic manifestations mimicking central nervous system infection or cranial nerve palsy.

摘要

孤立性蝶窦炎是一种罕见的疾病,由于其靠近眼眶和颅内区域,可能会出现严重并发症。我们报告一名13岁男孩因不明原因发热导致感染性休克住院。后来发现有面瘫。脑部磁共振成像显示蝶窦有肿物,右侧海绵窦和颈内静脉血栓形成。活检显示为慢性鼻窦炎。经切开引流手术和抗生素治疗后完全康复。急性蝶窦炎应纳入对模拟中枢神经系统感染或颅神经麻痹的感染表现的鉴别诊断中。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/c1f4/6334571/4857dbbcf864/TCMJ-31-63-g001.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/c1f4/6334571/4857dbbcf864/TCMJ-31-63-g001.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/c1f4/6334571/4857dbbcf864/TCMJ-31-63-g001.jpg

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本文引用的文献

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Non-Catheter-related Venous Thromboembolism in Children: Imaging Review from Head to Toe.儿童非导管相关静脉血栓栓塞症:从头到脚的影像学综述
Radiographics. 2017 Oct;37(6):1753-1774. doi: 10.1148/rg.2017170036.
2
Isolated acute sphenoid sinusitis presenting with hemicranial headache and ipsilateral abducens nerve palsy.孤立性急性蝶窦炎表现为半侧头痛和同侧展神经麻痹。
BMJ Case Rep. 2015 Jun 8;2015:bcr2015209408. doi: 10.1136/bcr-2015-209408.
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Unusual presentation of pediatric acute sphenoid sinusitis.小儿急性蝶窦炎的不典型表现。
Ann R Coll Surg Engl. 2022 Sep;104(8):e239-e243. doi: 10.1308/rcsann.2021.0338. Epub 2022 Apr 21.
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Int J Pediatr Otorhinolaryngol. 2006 Dec;70(12):2027-31. doi: 10.1016/j.ijporl.2006.07.011. Epub 2006 Aug 22.
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Isolated inflammatory sphenoid sinus disease: a revisitation of computed tomography indications based on presenting findings.孤立性炎性蝶窦疾病:基于临床表现对计算机断层扫描指征的再探讨。
Am J Rhinol. 2005 Nov-Dec;19(6):627-32.
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Complications of acute sinusitis in children.儿童急性鼻窦炎的并发症
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