• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利:CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验

中重型再生障碍性贫血的鉴别特征与共性。

Distinctive and common features of moderate aplastic anaemia.

机构信息

Department of Translational Hematology and Oncology Research, Taussig Cancer Institute, Cleveland Clinic, Cleveland, OH, USA.

Leukemia Program, Department of Hematology and Medical Oncology, Taussig Cancer Institute, Cleveland Clinic, Cleveland, OH, USA.

出版信息

Br J Haematol. 2020 Jun;189(5):967-975. doi: 10.1111/bjh.16460. Epub 2020 Jan 31.

DOI:10.1111/bjh.16460
PMID:32004386
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC8340733/
Abstract

The therapy algorithm for severe aplastic anaemia (sAA) is established but moderate AA (mAA), which likely reflects a more diverse pathogenic mechanism, often represents a treatment/management conundrum. A cohort of AA patients (n = 325) was queried for those with non-severe disease using stringent criteria including bone marrow hypocellularity and chronic persistence of moderately depressed blood counts. As a result, we have identified and analyzed pathological and clinical features in 85 mAA patients. Progression to sAA and direct clonal evolution (paroxysmal nocturnal haemoglobinuria/acute myeloid leukaemia; PNH/AML) occurred in 16%, 11% and 1% of mAA cases respectively. Of the mAA patients who received immunosuppressive therapy, 67% responded irrespective of time of initiation of therapy while conservatively managed patients showed no spontaneous remissions. Genomic analysis of mAA identified evidence of clonal haematopoiesis with both persisting and remitting patterns at low allelic frequencies; with more pronounced mutational burden in sAA. Most of the mAA patients have autoimmune pathogenesis similar to those with sAA, but mAA contains a mix of patients with diverse aetiologies. Although progression rates differed between mAA and sAA (P = 0·003), cumulative incidences of mortalities were only marginally different (P = 0·095). Our results provide guidance for diagnosis/management of mAA, a condition for which no current standard of care is established.

摘要

再生障碍性贫血(AA)的治疗方案已经建立,但中度 AA(mAA)可能反映了更具多样性的发病机制,通常代表了治疗/管理的难题。我们对一组 AA 患者(n=325)进行了查询,以确定那些符合严格标准(包括骨髓细胞减少症和中度血细胞计数持续减少)的非严重疾病患者。结果,我们在 85 例 mAA 患者中确定并分析了病理和临床特征。mAA 患者分别有 16%、11%和 1%进展为 sAA 和直接克隆进化(阵发性睡眠性血红蛋白尿/急性髓系白血病;PNH/AML)。接受免疫抑制治疗的 mAA 患者中,67%的患者有反应,而不管治疗开始的时间如何,而保守治疗的患者则没有自发缓解。mAA 的基因组分析发现了克隆性造血的证据,具有持续和缓解模式,等位基因频率较低;sAA 的突变负担更为明显。大多数 mAA 患者具有与 sAA 相似的自身免疫发病机制,但 mAA 包含了具有不同病因的患者混合。尽管 mAA 和 sAA 之间的进展率不同(P=0·003),但死亡率的累积发生率仅略有差异(P=0·095)。我们的研究结果为 mAA 的诊断/管理提供了指导,目前尚未确定 mAA 的标准治疗方法。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/f365920d72e1/BJH-189-967-g001.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/24f631bd8c42/BJH-189-967-g002.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/09fa1dc16ced/BJH-189-967-g003.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/f365920d72e1/BJH-189-967-g001.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/24f631bd8c42/BJH-189-967-g002.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/09fa1dc16ced/BJH-189-967-g003.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1ba0/9290125/f365920d72e1/BJH-189-967-g001.jpg

相似文献

1
Distinctive and common features of moderate aplastic anaemia.中重型再生障碍性贫血的鉴别特征与共性。
Br J Haematol. 2020 Jun;189(5):967-975. doi: 10.1111/bjh.16460. Epub 2020 Jan 31.
2
Secondary myelodysplastic syndrome and leukemia in acquired aplastic anemia and paroxysmal nocturnal hemoglobinuria.获得性再生障碍性贫血和阵发性睡眠性血红蛋白尿症中的继发性骨髓增生异常综合征和白血病。
Blood. 2020 Jul 2;136(1):36-49. doi: 10.1182/blood.2019000940.
3
Cell cycling stress in the monocyte line as a risk factor for progression of the aplastic anaemia/paroxysmal nocturnal haemoglobinuria syndrome to myelodysplastic syndrome.单核细胞系中的细胞周期应激作为再生障碍性贫血/阵发性睡眠性血红蛋白尿综合征进展为骨髓增生异常综合征的一个危险因素。
Acta Haematol. 2000;103(1):33-40. doi: 10.1159/000041002.
4
Guidelines for the diagnosis and management of adult aplastic anaemia.成人再生障碍性贫血诊断与治疗指南。
Br J Haematol. 2016 Jan;172(2):187-207. doi: 10.1111/bjh.13853. Epub 2015 Nov 16.
5
Long-term follow-up of clonal evolutions in 802 aplastic anemia patients: a single-center experience.802 例再生障碍性贫血患者克隆演变的长期随访:单中心经验。
Ann Hematol. 2011 May;90(5):529-37. doi: 10.1007/s00277-010-1140-9. Epub 2011 Jan 5.
6
Polyclonal hematopoiesis maintained in patients with bone marrow failure harboring a minor population of paroxysmal nocturnal hemoglobinuria-type cells.骨髓衰竭患者中存在少量阵发性睡眠性血红蛋白尿型细胞,其多克隆造血得以维持。
Blood. 2003 Aug 15;102(4):1211-6. doi: 10.1182/blood-2002-12-3706. Epub 2003 Apr 3.
7
Burden of illness among patients with severe aplastic anemia who have had insufficient response to immunosuppressive therapy: a multicenter retrospective chart review study.免疫抑制治疗反应不足的重型再生障碍性贫血患者的疾病负担:一项多中心回顾性图表审查研究。
Ann Hematol. 2020 Apr;99(4):743-752. doi: 10.1007/s00277-019-03809-5. Epub 2020 Feb 17.
8
A cohort study of the nature of paroxysmal nocturnal hemoglobinuria clones and PIG-A mutations in patients with aplastic anemia.再生障碍性贫血患者阵发性夜间血红蛋白尿克隆性质及PIG-A突变的队列研究。
Eur J Haematol. 2006 Jun;76(6):502-9. doi: 10.1111/j.0902-4441.2005.t01-1-EJH2467.x. Epub 2006 Mar 9.
9
Eltrombopag restores trilineage hematopoiesis in refractory severe aplastic anemia that can be sustained on discontinuation of drug.依鲁替尼可恢复对药物停药后可维持缓解的难治性重型再生障碍性贫血的三系造血。
Blood. 2014 Mar 20;123(12):1818-25. doi: 10.1182/blood-2013-10-534743. Epub 2013 Dec 17.
10
Clinical and prognostic significance of small paroxysmal nocturnal hemoglobinuria clones in myelodysplastic syndrome and aplastic anemia.骨髓增生异常综合征和再生障碍性贫血中小阵发性睡眠性血红蛋白尿克隆的临床和预后意义。
Leukemia. 2021 Nov;35(11):3223-3231. doi: 10.1038/s41375-021-01190-9. Epub 2021 Mar 4.

引用本文的文献

1
Analysis of the efficacy of avatrombopag for the delayed platelet engraftment after allogeneic hematopoietic stem cell transplantation for aplastic anemia.阿伐曲泊帕治疗再生障碍性贫血异基因造血干细胞移植后血小板延迟植入的疗效分析。
Front Med (Lausanne). 2025 Aug 8;12:1626325. doi: 10.3389/fmed.2025.1626325. eCollection 2025.
2
Effective treatment of refractory aplastic anemia with romiplostim after failure of multiple thrombopoietin receptor agonists: a single-center retrospective study.多种血小板生成素受体激动剂治疗失败后使用罗米司亭有效治疗难治性再生障碍性贫血:一项单中心回顾性研究
Ann Med. 2025 Dec;57(1):2514791. doi: 10.1080/07853890.2025.2514791. Epub 2025 Jun 19.
3

本文引用的文献

1
Consequences of mutant TET2 on clonality and subclonal hierarchy.突变型 TET2 对克隆性和亚克隆层次结构的影响。
Leukemia. 2018 Aug;32(8):1751-1761. doi: 10.1038/s41375-018-0150-9. Epub 2018 May 24.
2
Fanconi Anemia germline variants as susceptibility factors in aplastic anemia, MDS and AML.范可尼贫血种系变异作为再生障碍性贫血、骨髓增生异常综合征和急性髓系白血病的易感性因素。
Oncotarget. 2017 Dec 16;9(2):2050-2057. doi: 10.18632/oncotarget.23328. eCollection 2018 Jan 5.
3
Origins of myelodysplastic syndromes after aplastic anemia.再生障碍性贫血后骨髓增生异常综合征的起源
Clinical usefulness of next-generation sequencing-based target gene sequencing in diagnosis of inherited bone marrow failure syndrome.
基于下一代测序的靶基因测序在遗传性骨髓衰竭综合征诊断中的临床应用价值
Ann Hematol. 2025 May 13. doi: 10.1007/s00277-025-06392-0.
4
Initial management of patients with acquired aplastic anemia in the United States: results from a large national claims database.美国获得性再生障碍性贫血患者的初始管理:来自一个大型全国索赔数据库的结果。
Ann Hematol. 2025 Apr;104(4):2507-2515. doi: 10.1007/s00277-025-06307-z. Epub 2025 Mar 19.
5
Monitoring and Treatment of Paroxysmal Nocturnal Hemoglobinuria in Patients with Aplastic Anemia in Asia: An Expert Consensus.亚洲再生障碍性贫血患者阵发性睡眠性血红蛋白尿症的监测和治疗:专家共识。
Int J Mol Sci. 2024 Nov 13;25(22):12160. doi: 10.3390/ijms252212160.
6
Long-Term Follow-Up of Eltrombopag Treatment for Patients with Cyclosporin A Refractory/Relapsed Transfusion-Dependent Non-Severe Aplastic Anemia: A Report from a Single Center in China.艾曲泊帕治疗环孢素A难治/复发的输血依赖型非重型再生障碍性贫血患者的长期随访:来自中国单中心的报告
Acta Haematol. 2025;148(3):352-361. doi: 10.1159/000539905. Epub 2024 Jul 17.
7
A multicentre ambispective observational study into the incidence and clinical management of aplastic anaemia in Spain (IMAS study).一项关于西班牙再生障碍性贫血发病率和临床管理的多中心前瞻性观察研究(IMAS 研究)。
Ann Hematol. 2024 Mar;103(3):705-713. doi: 10.1007/s00277-023-05602-x. Epub 2024 Jan 4.
8
Deciphering treatment patterns in non-severe/moderate aplastic anemia: an international observational study.解读非重型/中型再生障碍性贫血的治疗模式:一项国际观察性研究。
Leukemia. 2023 Dec;37(12):2479-2485. doi: 10.1038/s41375-023-02047-z. Epub 2023 Oct 4.
9
Acquired Aplastic Anemia as a Clonal Disorder of Hematopoietic Stem Cells.获得性再生障碍性贫血作为造血干细胞的克隆性疾病。
Stem Cell Rev Rep. 2020 Jun;16(3):472-481. doi: 10.1007/s12015-020-09971-y.
Blood. 2017 Oct 26;130(17):1953-1957. doi: 10.1182/blood-2017-02-767731. Epub 2017 Sep 11.
4
Genomic determinants of chronic myelomonocytic leukemia.慢性粒单核细胞白血病的基因组决定因素。
Leukemia. 2017 Dec;31(12):2815-2823. doi: 10.1038/leu.2017.164. Epub 2017 May 30.
5
Long-term outcomes of 95 children with moderate aplastic anemia treated with horse antithymocyte globulin and cyclosporine.95例接受马抗胸腺细胞球蛋白和环孢素治疗的中度再生障碍性贫血患儿的长期预后
Pediatr Blood Cancer. 2017 May;64(5). doi: 10.1002/pbc.26305. Epub 2016 Nov 3.
6
Clonal hematopoiesis in acquired aplastic anemia.获得性再生障碍性贫血中的克隆性造血
Blood. 2016 Jul 21;128(3):337-47. doi: 10.1182/blood-2016-01-636381. Epub 2016 Apr 27.
7
Somatic Mutations and Clonal Hematopoiesis in Aplastic Anemia.再生障碍性贫血中的体细胞突变与克隆性造血
N Engl J Med. 2015 Oct 22;373(17):1675-6. doi: 10.1056/NEJMc1509703.
8
Genomic patterns associated with hypoplastic compared to hyperplastic myelodysplastic syndromes.与增生性骨髓增生异常综合征相比,发育不全相关的基因组模式。
Haematologica. 2015 Nov;100(11):e434-7. doi: 10.3324/haematol.2015.130112. Epub 2015 Aug 13.
9
Somatic Mutations and Clonal Hematopoiesis in Aplastic Anemia.再生障碍性贫血中的体细胞突变与克隆性造血
N Engl J Med. 2015 Jul 2;373(1):35-47. doi: 10.1056/NEJMoa1414799.
10
Emergence of clonal hematopoiesis in the majority of patients with acquired aplastic anemia.大多数获得性再生障碍性贫血患者出现克隆性造血。
Cancer Genet. 2015 Apr;208(4):115-28. doi: 10.1016/j.cancergen.2015.01.007. Epub 2015 Feb 2.