Pediatric Radiology Department, Hospital Necker-Enfants Malades, AP-HP, Paris, France.
Pediatric Nephrology Department, Hospital Necker-Enfants Malades, AP-HP, Paris, France.
Pediatr Nephrol. 2020 Jun;35(6):1033-1040. doi: 10.1007/s00467-020-04480-z. Epub 2020 Feb 10.
While typical ultrasound patterns of ciliopathy-related cystic kidney diseases have been described in children, ultrasound findings can overlap between different diseases and atypical patterns exist. In this study, we assessed the presence of the "salt and pepper" pattern in different renal ciliopathies and looked for additional ultrasound features.
This single-center, retrospective study included all patients with a molecular-proven diagnosis of renal ciliopathy, referred to our center between 2007 and 2017. Images from the first and follow-up ultrasound exams were reviewed. Basic ultrasound features were grouped into patterns and compared to genetic diagnoses. The "salt and pepper" aspect was described as enlarged kidneys with heterogeneous, increased parenchymal echogenicity.
A total of 41 children with 5 different renal ciliopathies were included (61% male; median age, 6 years [range, 3 days to 17 years]). The "salt and pepper" pattern was present in 14/15 patients with an autosomal recessive polycystic kidney disease (ARPKD). A similar pattern was found in 1/4 patients with an autosomal dominant polycystic kidney disease and in 1/11 patients with HNF1B mutation. Additional signs found were areas of cortical sparing, comet-tail artifacts, and color comet-tail artifacts.
Although the "salt and pepper" ultrasound pattern is predominantly found in ARPKD, it may be detected in other ciliopathies. The color comet-tail artifact is an interesting sign when suspecting a renal ciliopathy in case of enlarged hyperechoic kidneys with no detectable microcysts on B-mode grayscale ultrasound.
虽然已有描述过与纤毛病相关的囊性肾病的典型超声模式,但不同疾病之间的超声表现可能会有重叠,而且存在不典型的模式。在这项研究中,我们评估了不同肾纤毛病中“盐和胡椒”模式的存在情况,并寻找了其他超声特征。
这是一项单中心、回顾性研究,纳入了 2007 年至 2017 年间在我们中心被诊断为肾纤毛病的所有患者,这些患者均具有分子学确诊结果。我们回顾了首次和随访超声检查的图像。将基本超声特征分为不同的模式,并与基因诊断进行比较。“盐和胡椒”外观被描述为肾脏增大,实质回声不均匀增强。
共纳入了 41 名患有 5 种不同肾纤毛病的儿童(61%为男性;中位年龄为 6 岁[范围为 3 天至 17 岁])。15 名常染色体隐性多囊肾病(ARPKD)患者中有 14 名存在“盐和胡椒”模式。4 名常染色体显性多囊肾病患者中有 1 名和 11 名 HNF1B 突变患者中有 1 名存在类似的模式。还发现了其他征象,包括皮质保留区、彗星尾伪像和彩色彗星尾伪像。
尽管“盐和胡椒”超声模式主要见于 ARPKD,但也可能在其他纤毛病中发现。当怀疑存在肾纤毛病时,在 B 型灰阶超声上未见微囊且肾脏增大呈高回声时,彩色彗星尾伪像则是一个有趣的征象。