Hirt Penelope, Paul Suchismita, Phuthongkam Weena, Schachner Lawrence
All authors are with the Department of Dermatology and Cutaneous Surgery at the University of Miami, Miller School of Medicine in Miami, Florida.
Dr. Phuthongkam is also with the Department of Pediatrics at the Faculty of Medicine Vajira Hospital at Navamindradhiraj University in Bangkok, Thailand.
J Clin Aesthet Dermatol. 2020 Jan;13(1):38-40. Epub 2020 Jan 1.
Oral mucosal involvement in patients with morphea is quite rare. Unilateral nevoid telangiectasia is a rare vascular dermatosis characterized by unilateral telangiectasia distributed in a dermatomal pattern, especially on the upper trunk and extremities. We describe a case of a 10-year-old female patient that presents with morphea on her left chin and upper lip extending to the inner oral mucosa as well as a unilateral nevoid telangiectasia on her left cheek as an early presentation of localized scleroderma. This case is significant as it demonstrates a striking clinical presentation of morphea and an interesting early presentation of morphea as a unilateral nevoid telangiectasia that improved after treatment with oral methotrexate and prednisone.
硬斑病患者出现口腔黏膜受累的情况相当罕见。单侧痣样毛细血管扩张症是一种罕见的血管性皮肤病，其特征为单侧毛细血管扩张呈皮节分布，尤其见于上躯干和四肢。我们报告一例10岁女性患者，其左侧下巴和上唇出现硬斑病，并延伸至口腔内侧黏膜，同时左侧脸颊有单侧痣样毛细血管扩张症，这是局限性硬皮病的早期表现。该病例意义重大，因为它展示了硬斑病显著的临床表现，以及硬斑病作为单侧痣样毛细血管扩张症这一有趣的早期表现，经口服甲氨蝶呤和泼尼松治疗后病情有所改善。
