Institute for Medical Informatics and Biometry (IMB), Carl Gustav Carus Faculty of Medicine, Technische Universität Dresden, Dresden, Germany.
Division of Stem Cells and Cancer, German Cancer Research Center (DKFZ), Heidelberg, Germany.
Sci Rep. 2020 Jul 29;10(1):12761. doi: 10.1038/s41598-020-69691-8.
Acute myeloid leukemia (AML) is a very heterogeneous and highly malignant blood cancer. Mutations of the DNA methyltransferase DNMT3A are among the most frequent recurrent genetic lesions in AML. The majority of DNMT3A-mutant AML patients shows fast relapse and poor survival, but also patients with long survival or long-term remission have been reported. Underlying molecular signatures and mechanisms that contribute to these survival differences are only poorly understood and have not been studied in detail so far. We applied hierarchical clustering to somatic gene mutation profiles of 51 DNMT3A-mutant patients from The Cancer Genome Atlas (TCGA) AML cohort revealing two robust patient subgroups with profound differences in survival. We further determined molecular signatures that distinguish both subgroups. Our results suggest that FLT3 and/or NPM1 mutations contribute to survival differences of DNMT3A-mutant patients. We observed an upregulation of genes of the p53, VEGF and DNA replication pathway and a downregulation of genes of the PI3K-Akt pathway in short- compared to long-lived patients. We identified that the majority of measured miRNAs was downregulated in the short-lived group and we found differentially expressed microRNAs between both subgroups that have not been reported for AML so far (miR-153-2, miR-3065, miR-95, miR-6718) suggesting that miRNAs could be important for prognosis. In addition, we learned gene regulatory networks to predict potential major regulators and found several genes and miRNAs with known roles in AML pathogenesis, but also interesting novel candidates involved in the regulation of hematopoiesis, cell cycle, cell differentiation, and immunity that may contribute to the observed survival differences of both subgroups and could therefore be important for prognosis. Moreover, the characteristic gene mutation and expression signatures that distinguished short- from long-lived patients were also predictive for independent DNMT3A-mutant AML patients from other cohorts and could also contribute to further improve the European LeukemiaNet (ELN) prognostic scoring system. Our study represents the first in-depth computational approach to identify molecular factors associated with survival differences of DNMT3A-mutant AML patients and could trigger additional studies to develop robust molecular markers for a better stratification of AML patients with DNMT3A mutations.
急性髓系白血病(AML)是一种非常异质性和高度恶性的血液系统恶性肿瘤。DNA 甲基转移酶 DNMT3A 的突变是 AML 中最常见的复发性遗传病变之一。大多数 DNMT3A 突变型 AML 患者表现为快速复发和不良生存,但也有报道长期生存或长期缓解的患者。导致这些生存差异的潜在分子特征和机制尚未得到很好的理解,迄今为止也没有进行详细研究。我们对来自癌症基因组图谱(TCGA)AML 队列的 51 名 DNMT3A 突变患者的体细胞基因突变谱进行了层次聚类,揭示了两组具有显著生存差异的稳健患者亚组。我们进一步确定了区分这两个亚组的分子特征。我们的结果表明,FLT3 和/或 NPM1 突变导致 DNMT3A 突变型患者的生存差异。与生存期长的患者相比,我们观察到短生存期患者中 p53、VEGF 和 DNA 复制途径的基因上调和 PI3K-Akt 途径的基因下调。我们发现,在短生存期组中,大多数测量的 miRNA 下调,并且我们发现两个亚组之间存在差异表达的 microRNA,迄今为止尚未报道 AML 中的 microRNA(miR-153-2、miR-3065、miR-95、miR-6718),这表明 miRNA 可能对预后很重要。此外,我们学习了基因调控网络以预测潜在的主要调节剂,并发现了一些在 AML 发病机制中具有已知作用的基因和 miRNA,以及一些有趣的新候选物,它们参与了造血、细胞周期、细胞分化和免疫的调节,这可能有助于两个亚组的观察到的生存差异,并因此可能对预后很重要。此外,区分短生存期和长生存期患者的特征性基因突变和表达特征也可预测来自其他队列的独立 DNMT3A 突变 AML 患者,并且还可以帮助进一步改进欧洲白血病网络(ELN)预后评分系统。我们的研究代表了首次深入的计算方法来确定与 DNMT3A 突变型 AML 患者生存差异相关的分子因素,并可能引发进一步的研究,以开发稳健的分子标志物,更好地对 DNMT3A 突变的 AML 患者进行分层。