Martellucci Salvatore, Castellucci Andrea, Malara Pasquale, Pagliuca Giulio, Clemenzi Veronica, Stolfa Andrea, Gallo Andrea, Libonati Giacinto Asprella
ENT Unit, Santa Maria Goretti Hospital, AUSL Latina, Italy.
ENT Unit, Arcispedale Santa Maria Nuova, AUSL-IRCCS, Reggio Emilia, Italy.
J Audiol Otol. 2022 Jan;26(1):55-60. doi: 10.7874/jao.2020.00507. Epub 2021 Feb 15.
Spontaneous canalith jam is an uncommon form of benign paroxysmal positional vertigo mimicking acute vestibular neuritis. We described for the first time a spontaneous horizontal semicircular canalith jam associated with a typical canalolithiasis involving contralateral posterior semicircular canal (PSC), illustrating how the latter condition modified direction-fixed nystagmus during head movements. An 81-year-old woman with persistent vertigo referred to our center. Video-Frenzel examination showed horizontal direction-fixed right-beating nystagmus in primary gaze position, inhibited by visual fixation. She exhibited corrective saccades after leftward head impulses. Chin-to-chest positioning at the head-pitch test did not modify spontaneous nystagmus, whereas slight torsional components with the top pole of the eye beating toward the right ear appeared in backward head-bending, resulting in mixed horizontal-torsional nystagmus. At supine positioning tests, direction-fixed nystagmus turned into direction-changing geotropic horizontal nystagmus, which was stronger on the left side, while overlapping upbeat nystagmus with torsional right-beating components appeared on the right. Primary clinical findings were consistent with a left horizontal semicircular canalith jam, inducing a persistent utriculofugal cupular displacement, combined with a typical right-sided PSC-canalolithiasis. Once canalith jam crumbled, resulting in a non-ampullary arm canalolithiasis of the horizontal semicircular canal, both involved canals were freed by debris with appropriate repositioning procedures.
自发性管结石嵌塞是一种罕见的良性阵发性位置性眩晕形式,可模拟急性前庭神经炎。我们首次描述了一种与对侧后半规管(PSC)典型管结石症相关的自发性水平半规管管结石嵌塞,说明了后一种情况如何改变头部运动期间方向固定的眼球震颤。一名81岁患有持续性眩晕的女性转诊至我们中心。视频Frenzel检查显示,在初始注视位置存在水平方向固定的右眼跳动性眼球震颤,可被视觉注视抑制。她在向左头部脉冲后出现矫正性扫视。头部俯仰试验中下巴抵胸的姿势并未改变自发性眼球震颤,而在向后头部弯曲时,眼球顶部朝向右侧耳朵出现轻微扭转成分,导致混合性水平-扭转性眼球震颤。在仰卧位试验中,方向固定的眼球震颤转变为方向改变的地向性水平眼球震颤,左侧更强,而右侧出现重叠的向上跳动性眼球震颤和扭转性右眼跳动成分。主要临床发现与左水平半规管管结石嵌塞一致,导致持续性椭圆囊离壶腹性嵴帽移位,同时合并典型的右侧PSC管结石症。一旦管结石嵌塞破碎,导致水平半规管非壶腹臂管结石症,通过适当的重新定位程序,两个受累半规管都被碎片清除。