Callejas-Moraga Eduardo Luis, Guillén-Del-Castillo Alfredo, Perurena-Prieto Janire, Sanz-Martínez Maria Teresa, Fonollosa-Pla Vicente, Lorite-Gomez Karen, Severino Adriana, Bellocchi Chiara, Beretta Lorenzo, Mahler Michael, Simeón-Aznar Carmen P
Unit of Systemic Autoimmune Diseases, Department of Internal Medicine, Hospital Universitari Parc Taulí, Barcelona, Spain.
Unit of Systemic Autoimmune Diseases, Department of Internal Medicine, Hospital Universitari Vall d'Hebron, Barcelona, Spain.
Rheumatology (Oxford). 2021 Dec 24;61(1):154-162. doi: 10.1093/rheumatology/keab279.
To analyse the prevalence, the clinical characteristics, the overall survival and the event-free survival (EFS) of SSc patients who express anti-U11/U12 RNP (RNPC-3) antibodies.
A total of 447 SSc patients from Barcelona (n = 286) and Milan (n = 161) were selected. All samples were tested using a particle-based multi-analyte technology. We compared anti-RNPC-3 positive and negative patients. Epidemiological, clinical features and survival were analysed. End-stage lung disease (ESLD) was defined if the patient developed forced vital capacity <50% of predicted, needed oxygen therapy or lung transplantation. EFS was defined as the period of time free of either ESLD or death.
Nineteen of 447 (4.3%) patients had anti-RNPC-3 antibodies and interstitial lung disease (ILD) was more frequent (11, 57.9% vs 144, 33.6%, P =0.030) in individuals with anti-RNPC-3 antibodies. More patients reached ESLD in the positive group (7, 36.8% vs 74, 17.3%, P = 0.006), and a higher use of non-glucocorticoid immunosuppressive drugs was observed (11, 57.9% vs 130, 30.4%, P = 0.012). Anti-RNPC-3 positive patients had lower EFS, both in the total cohort (log-rank P =0.001), as well as in patients with ILD (log-rank P = 0.002). In multivariate Cox regression analysis, diffuse cutaneous subtype, age at onset, the presence of ILD or pulmonary arterial hypertension and the expression of anti-RNPC-3 positivity or anti-topo I were independently associated with worse EFS.
The presence of anti-RNPC-3 was associated with higher frequency of ILD and either ESLD or death. These data suggest anti-RNPC-3 is an independent poor prognosis antibody in SSc, especially if ILD is also present.
分析表达抗U11/U12 RNP(RNPC-3)抗体的系统性硬化症(SSc)患者的患病率、临床特征、总生存期和无事件生存期(EFS)。
选取来自巴塞罗那(n = 286)和米兰(n = 161)的447例SSc患者。所有样本均采用基于颗粒的多分析物技术进行检测。我们比较了抗RNPC-3阳性和阴性患者。分析了流行病学、临床特征和生存期。如果患者的用力肺活量(FVC)<预测值的50%、需要吸氧治疗或进行肺移植,则定义为终末期肺病(ESLD)。EFS定义为无ESLD或死亡的时间段。
447例患者中有19例(4.3%)抗RNPC-3抗体阳性,抗RNPC-3抗体阳性个体的间质性肺病(ILD)更为常见(11例,57.9% vs 144例,33.6%,P = 0.030)。阳性组中更多患者达到ESLD(7例,36.8% vs 74例,17.3%,P = 0.006),并且观察到非糖皮质激素免疫抑制药物的使用频率更高(11例,57.9% vs 130例,30.4%,P = 0.012)。抗RNPC-3阳性患者的EFS较低,在整个队列中(对数秩检验P = 0.001)以及ILD患者中(对数秩检验P = 0.002)均如此。在多变量Cox回归分析中,弥漫性皮肤亚型、发病年龄、ILD或肺动脉高压的存在以及抗RNPC-3阳性或抗拓扑异构酶I的表达与较差的EFS独立相关。
抗RNPC-3的存在与ILD以及ESLD或死亡的较高频率相关。这些数据表明抗RNPC-3是SSc中一个独立的预后不良抗体,尤其是在同时存在ILD的情况下。