Nagashima Yoshitaka, Nishimura Yusuke, Ito Hiroshi, Nishii Tomoya, Oyama Takahiro, Saito Ryuta
Department of Neurosurgery, Nagoya University School of Medicine, Nagoya, Aichi, Japan.
NMC Case Rep J. 2022 Sep 15;9:295-299. doi: 10.2176/jns-nmc.2022-0036. eCollection 2022.
Arachnoiditis ossificans (AO) is a rare disease, wherein ossified lesions in the subarachnoid space obstruct the flow of spinal fluid or compress the spinal cord, thereby causing myelopathy. Here we describe a rare case of AO and discuss the diagnosis and treatment strategies for this disease. A 66-year-old man with a history of subarachnoid hemorrhage presented with gait disturbance and dysuria for 7 months. Spinal magnetic resonance imaging and computed tomography (CT) myelography showed syringomyelia at the T5-T8 level and dorsally tethered spinal cord at the T8-T10 level. Preoperative noncontrast CT was not performed. The patient was diagnosed with adhesive arachnoiditis and underwent arachnoidolysis. However, intraoperative findings showed the presence of ossification lesions on the dorsal surface of the spinal cord, and intraoperative ultrasound (IOU) showed a hyperintense lesion with acoustic shadowing on the dorsal surface of the spinal cord, with limited visibility of the spinal cord. After removal of the lesions, IOU showed untethered and well-decompressed spinal cord and restoration of cerebrospinal fluid pulsation. Based on these findings, the patient was finally diagnosed with AO, which is an extremely rare disease, with an unknown frequency of occurrence. Therefore, all patients with adhesive spinal arachnoiditis require a preoperative noncontrast CT scan to evaluate for ossification lesions. In this case, we were fortunate to be able to treat AO with IOU, which demonstrated specific findings.
骨化性蛛网膜炎(AO)是一种罕见疾病,其中蛛网膜下腔的骨化性病变会阻碍脑脊液流动或压迫脊髓,从而导致脊髓病。在此,我们描述一例罕见的AO病例,并讨论该疾病的诊断和治疗策略。一名有蛛网膜下腔出血病史的66岁男性,出现步态障碍和排尿困难7个月。脊髓磁共振成像和计算机断层扫描(CT)脊髓造影显示T5 - T8水平存在脊髓空洞症,T8 - T10水平脊髓背侧受牵拉。未进行术前平扫CT检查。该患者被诊断为粘连性蛛网膜炎并接受了蛛网膜松解术。然而,术中发现脊髓背侧存在骨化病变,术中超声(IOU)显示脊髓背侧有高回声病变且伴有声影,脊髓可视性受限。切除病变后,IOU显示脊髓不再受牵拉且减压良好,脑脊液搏动恢复。基于这些发现,该患者最终被诊断为AO,这是一种极其罕见的疾病,发病率未知。因此,所有粘连性脊髓蛛网膜炎患者术前都需要进行平扫CT扫描以评估是否存在骨化病变。在本病例中,我们有幸能够通过IOU对AO进行治疗,其显示出了特异性表现。