University of KwaZulu-Natal - Department of Hematology, National Health Laboratory Services, School of laboratory medicine, Durban, South Africa.
Inkosi Albert Luthuli Central Hospital, Durban, South Africa.
J Prim Care Community Health. 2023 Jan-Dec;14:21501319231194970. doi: 10.1177/21501319231194970.
In acquired hemophilia A (AHA), the body produces auto-antibodies against Factor VIII. Although AHA is rare, with an incidence of 1.5 patients/1 million population/year, there is a strong association with human immunodeficiency virus (HIV) infection. The accurate interpretation of screening coagulation tests is critical to identify patients with AHA, as the mortality rate secondary to bleeding is high.
This was a retrospective case series which included all newly diagnosed AHA patients that were referred to Hemophilia care unit at King Edward VIII Hospital, Durban, South Africa from January 2011 to December 2021. The clinical presentation and laboratory results were documented.
Five patients were included in this case series. All patients were females aged between 28 and 64 years of age and they were HIV seropositive. They presented with spontaneous cutaneous and intramuscular bleeding. Four patients were virologically suppressed on anti-retroviral therapy, and no patient had a family history of congenital bleeding diathesis. Laboratory investigations confirmed AHA with high Factor VIII inhibitor titers, which ranged from 41 to 900 Bethesda Units (BU). All patients were managed with bypassing agents and oral corticosteroids. The monitoring of patients after the initiation of treatment was difficult as they all defaulted treatment.
In view of the prevalence of HIV in sub-Saharan Africa, there is a possibility that AHA is under-diagnosed in our setting. The clinician and the laboratory have a combined critical role in identifying patients with AHA as the investigation of a prolonged APTT is mandatory. There are challenges in managing AHA patients in a resource-constrained setting.
获得性血友病 A(AHA)中,机体产生针对因子 VIII 的自身抗体。尽管 AHA 较为罕见,发病率为 1.5 例/100 万人群/年,但与人类免疫缺陷病毒(HIV)感染密切相关。准确解读筛选性凝血试验对于识别 AHA 患者至关重要,因为出血导致的死亡率很高。
这是一项回顾性病例系列研究,纳入了 2011 年 1 月至 2021 年 12 月期间南非德班爱德华七世国王医院血友病护理病房转诊的所有新诊断为 AHA 的患者。记录了患者的临床表现和实验室结果。
本病例系列纳入了 5 例患者,均为年龄 28 至 64 岁的女性,HIV 血清阳性。她们表现为自发性皮肤和肌肉内出血。4 例患者接受抗逆转录病毒治疗后病毒学抑制,且无患者有先天性出血性疾病家族史。实验室检查证实 AHA 伴高因子 VIII 抑制剂滴度,范围为 41 至 900 贝塞斯达单位(BU)。所有患者均接受了旁路制剂和口服皮质类固醇治疗。由于所有患者均停止治疗,因此在开始治疗后对患者的监测较为困难。
鉴于撒哈拉以南非洲 HIV 的流行,我们的环境中可能存在 AHA 漏诊的情况。临床医生和实验室在识别 AHA 患者方面具有共同的关键作用,因为必须对延长的 APTT 进行调查。在资源有限的环境中管理 AHA 患者存在挑战。