Goldberg Alexander R, Dovas Athanassios, Torres Daniela, Sharma Sohani Das, Mela Angeliki, Merricks Edward M, Olabarria Markel, Shokooh Leila Abrishami, Zhao Hanzhi T, Kotidis Corina, Calvaresi Peter, Viswanathan Ashwin, Banu Matei A, Razavilar Aida, Sudhakar Tejaswi D, Saxena Ankita, Chokran Cole, Humala Nelson, Mahajan Aayushi, Xu Weihao, Metz Jordan B, Chen Cady, Bushong Eric A, Boassa Daniela, Ellisman Mark H, Hillman Elizabeth M C, McKhann Guy M, Gill Brian J A, Rosenfeld Steven S, Schevon Catherine A, Bruce Jeffrey N, Sims Peter A, Peterka Darcy S, Canoll Peter
Department of Pathology and Cell Biology, Irving Cancer Research Center, Columbia University Irving Medical Center, New York, NY 10032, USA.
Department of Systems Biology, Columbia University Irving Medical Center, New York, NY 10032.
bioRxiv. 2024 Jan 21:2024.01.10.575092. doi: 10.1101/2024.01.10.575092.
Gliomas are highly aggressive brain tumors characterized by poor prognosis and composed of diffusely infiltrating tumor cells that intermingle with non-neoplastic cells in the tumor microenvironment, including neurons. Neurons are increasingly appreciated as important reactive components of the glioma microenvironment, due to their role in causing hallmark glioma symptoms, such as cognitive deficits and seizures, as well as their potential ability to drive glioma progression. Separately, mTOR signaling has been shown to have pleiotropic effects in the brain tumor microenvironment, including regulation of neuronal hyperexcitability. However, the local cellular-level effects of mTOR inhibition on glioma-induced neuronal alterations are not well understood. Here we employed neuron-specific profiling of ribosome-bound mRNA via 'RiboTag,' morphometric analysis of dendritic spines, and in vivo calcium imaging, along with pharmacological mTOR inhibition to investigate the impact of glioma burden and mTOR inhibition on these neuronal alterations. The RiboTag analysis of tumor-associated excitatory neurons showed a downregulation of transcripts encoding excitatory and inhibitory postsynaptic proteins and dendritic spine development, and an upregulation of transcripts encoding cytoskeletal proteins involved in dendritic spine turnover. Light and electron microscopy of tumor-associated excitatory neurons demonstrated marked decreases in dendritic spine density. In vivo two-photon calcium imaging in tumor-associated excitatory neurons revealed progressive alterations in neuronal activity, both at the population and single-neuron level, throughout tumor growth. This in vivo calcium imaging also revealed altered stimulus-evoked somatic calcium events, with changes in event rate, size, and temporal alignment to stimulus, which was most pronounced in neurons with high-tumor burden. A single acute dose of AZD8055, a combined mTORC1/2 inhibitor, reversed the glioma-induced alterations on the excitatory neurons, including the alterations in ribosome-bound transcripts, dendritic spine density, and stimulus evoked responses seen by calcium imaging. These results point to mTOR-driven pathological plasticity in neurons at the infiltrative margin of glioma - manifested by alterations in ribosome-bound mRNA, dendritic spine density, and stimulus-evoked neuronal activity. Collectively, our work identifies the pathological changes that tumor-associated excitatory neurons experience as both hyperlocal and reversible under the influence of mTOR inhibition, providing a foundation for developing therapies targeting neuronal signaling in glioma.
胶质瘤是高度侵袭性的脑肿瘤,预后较差,由弥漫性浸润的肿瘤细胞组成,这些细胞与肿瘤微环境中的非肿瘤细胞(包括神经元)相互混合。由于神经元在引起胶质瘤标志性症状(如认知缺陷和癫痫发作)方面的作用,以及它们驱动胶质瘤进展的潜在能力,神经元越来越被视为胶质瘤微环境的重要反应成分。另外,mTOR信号通路已被证明在脑肿瘤微环境中具有多效性作用,包括调节神经元的过度兴奋。然而,mTOR抑制对胶质瘤诱导的神经元改变的局部细胞水平影响尚不清楚。在这里,我们通过“RiboTag”对核糖体结合mRNA进行神经元特异性分析、对树突棘进行形态计量分析和体内钙成像,并结合药理学mTOR抑制,来研究胶质瘤负荷和mTOR抑制对这些神经元改变的影响。对肿瘤相关兴奋性神经元的RiboTag分析显示,编码兴奋性和抑制性突触后蛋白以及树突棘发育的转录本下调,而编码参与树突棘周转的细胞骨架蛋白的转录本上调。对肿瘤相关兴奋性神经元的光镜和电镜检查显示树突棘密度显著降低。在肿瘤相关兴奋性神经元中进行的体内双光子钙成像显示,在肿瘤生长的整个过程中,在群体和单细胞水平上神经元活动都有渐进性改变。这种体内钙成像还揭示了刺激诱发的体细胞钙事件的改变,包括事件发生率、大小和与刺激的时间对齐的变化,这在肿瘤负荷高的神经元中最为明显。单次急性剂量的AZD8055(一种mTORC1/2联合抑制剂)逆转了胶质瘤诱导的兴奋性神经元改变,包括核糖体结合转录本、树突棘密度和钙成像所见的刺激诱发反应的改变。这些结果表明,在胶质瘤浸润边缘的神经元中存在mTOR驱动的病理可塑性,表现为核糖体结合mRNA、树突棘密度和刺激诱发的神经元活动的改变。总的来说,我们的工作确定了肿瘤相关兴奋性神经元在mTOR抑制影响下经历的病理变化既是超局部的又是可逆的,为开发针对胶质瘤中神经元信号传导的治疗方法提供了基础。