Division of Immunology & Allergy, Department of Pediatrics, Hospital for Sick Children, University of Toronto, Toronto, ON M5S 1A1, Canada.
Department of Pediatrics, King Faisal Specialist Hospital and Research Center Ar Rawdah, Jeddah 23433, Saudi Arabia.
Genes (Basel). 2024 Jul 15;15(7):920. doi: 10.3390/genes15070920.
Severe combined immunodeficiency (SCID) is a life-threatening genetic disorder caused by critical defects of the immune system. Almost all cases are lethal if not treated within the first two years of life. Early diagnosis and intervention are thus essential for improving patient outcomes. In 2013, Ontario became the first Canadian province to perform newborn screening (NBS) for SCID by T cell receptor excision circles (TRECs) analysis, a surrogate marker of thymic function and lymphocyte maturation.
This retrospective study reports on nearly 10 years of NBS for SCID at a quaternary referral centre.
From August 2013 to April 2023, our centre's densely populated catchment area flagged 162 newborns with low TRECs levels, including 10 cases with SCID. Follow-up revealed other causes of low TRECs, including non-SCID T cell lymphopenia (secondary/reversible or idiopathic causes, and syndromic conditions) and prematurity. A small number of cases with normal repeat TRECs levels and/or T cell subsets were also flagged. Province-wide data from around this period revealed at least 24 diagnosed cases of SCID or Leaky SCID.
This is the first report of NBS outcomes in a Canadian province describing the causative genetic defects, and the non-SCID causes of a positive NBS for SCID.
严重联合免疫缺陷症(SCID)是一种危及生命的遗传性疾病,由免疫系统的严重缺陷引起。如果不在生命的头两年内得到治疗,几乎所有病例都是致命的。因此,早期诊断和干预对于改善患者的预后至关重要。2013 年,安大略省成为加拿大第一个通过 T 细胞受体切除环(TREC)分析对 SCID 进行新生儿筛查(NBS)的省份,TREC 是胸腺功能和淋巴细胞成熟的替代标志物。
本回顾性研究报告了在一家四级转诊中心进行近 10 年的 NBS 以筛查 SCID 的情况。
从 2013 年 8 月到 2023 年 4 月,我们中心人口密集的服务区域发现了 162 名 TREC 水平较低的新生儿,其中包括 10 例 SCID 患者。随访发现其他导致 TREC 水平降低的原因,包括非 SCID T 细胞淋巴细胞减少症(继发/可逆或特发性原因,以及综合征)和早产。少数 TREC 水平正常或 T 细胞亚群正常的病例也被标记出来。同期全省数据显示,至少有 24 例确诊的 SCID 或渗漏性 SCID 病例。
这是加拿大第一个报告 NBS 结果的省份,描述了导致 NBS 筛查 SCID 阳性的遗传缺陷和非 SCID 原因。