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干燥综合征患者合并细支气管腺瘤/纤毛黏液结节状乳头状瘤伴淋巴样间质性肺炎:一例报告及系统评价

Bronchiolar adenoma/ciliated muconodular papillary tumor complicated by lymphoid interstitial pneumonia in a patient with Sjögren's disease: A case report and systematic review.

作者信息

Çağan Pinar, Kimiaei Ali, Safaei Seyedehtina, Youcefi Houssam Eddine, Abu Saadeh Alara, Yaman Feride, Yapıcıer Özlem, Kutlu Cemal Asim

机构信息

Department of Thoracic Surgery, Bahçeşehir University, Istanbul, Turkey.

Department of Pulmonology, Bahçeşehir University, Istanbul, Turkey.

出版信息

Thorac Cancer. 2024 Oct;15(28):1975-1988. doi: 10.1111/1759-7714.15420. Epub 2024 Aug 18.

DOI:10.1111/1759-7714.15420
PMID:39155148
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC11444930/
Abstract

Bronchiolar adenoma (BA)/ciliated muconodular papillary tumor (CMPT) is a rare pulmonary neoplasm, with less than 150 cases documented in the literature. We report a unique case of BA/CMPT complicated by lymphoid interstitial pneumonia (LIP) in a 55-year-old male with Sjögren's disease. This is the first documented instance of such a comorbidity. Through a systematic review of PubMed, we also summarize the demographic, clinical, radiological, histopathological, and treatment characteristics of CMPT.

摘要

细支气管腺瘤(BA)/纤毛黏液结节状乳头状瘤(CMPT)是一种罕见的肺肿瘤,文献记载的病例不足150例。我们报告了一例55岁患有干燥综合征的男性患者,其BA/CMPT并发淋巴样间质性肺炎(LIP)。这是此类合并症的首例文献记载病例。通过对PubMed进行系统综述,我们还总结了CMPT的人口统计学、临床、放射学、组织病理学及治疗特征。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/851879ed07db/TCA-15-1975-g002.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/7ec4ca20d914/TCA-15-1975-g006.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/55d744a66875/TCA-15-1975-g007.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/76454f7e62bf/TCA-15-1975-g008.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/ff0c2ed0e01d/TCA-15-1975-g003.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/35e032995851/TCA-15-1975-g004.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/dc40e9afda3a/TCA-15-1975-g009.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/531d389d613f/TCA-15-1975-g005.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/851879ed07db/TCA-15-1975-g002.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/7ec4ca20d914/TCA-15-1975-g006.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/55d744a66875/TCA-15-1975-g007.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/76454f7e62bf/TCA-15-1975-g008.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/ff0c2ed0e01d/TCA-15-1975-g003.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/35e032995851/TCA-15-1975-g004.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/dc40e9afda3a/TCA-15-1975-g009.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/531d389d613f/TCA-15-1975-g005.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/36c9/11444930/851879ed07db/TCA-15-1975-g002.jpg

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本文引用的文献

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Ciliated Muconodular Papillary Tumors of the Lung Harboring Fusion: Case Report and Review of the Literature.肺的纤毛黏液结节乳头状肿瘤伴融合:病例报告及文献复习。
Int J Surg Pathol. 2024 Oct;32(7):1357-1363. doi: 10.1177/10668969241226707. Epub 2024 Feb 6.
2
Bronchiole adenoma/pulmonary ciliated mucinous nodular papillary tumor: Case series and literature review.细支气管腺瘤/肺纤毛黏液性结节性乳头状肿瘤:病例系列和文献复习。
Medicine (Baltimore). 2023 Dec 15;102(50):e36559. doi: 10.1097/MD.0000000000036559.
3
Bronchiolar adenoma/ciliated muconodular papillary tumour: advancing clinical, pathological, and imaging insights for future perspectives.
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