Sahu Animesh, Dalai Richie, Srivastava Saurav, Chowdhary Bhabesh K, Kumari Madhuri
Department of Neonatology, All India Institute of Medical Sciences, Patna, Patna, IND.
Department of Pediatric Surgery, All India Institute of Medical Sciences, Patna, Patna, IND.
Cureus. 2024 Nov 2;16(11):e72904. doi: 10.7759/cureus.72904. eCollection 2024 Nov.
A neonate with an antenatally detected mass in the coccygeal region experienced sudden abdominal worsening, with abdominal distension and bloody aspirates on day 4 of life. The abdominal radiograph revealed pneumatosis intestinalis (necrotizing enterocolitis stage IIa), requiring discontinuation of feeds and initiation of intravenous antibiotics. Computed tomography of the mass and abdomen showed that the coccygeal mass had an intra-abdominal extension, pushing the bowel loops and likely representing a Type II sacrococcygeal teratoma. Given the lesion's large size and vascularity, we hypothesize that chronic bowel compression with vascular steal may have contributed to gut ischemia, stasis, and subsequent necrotizing enterocolitis. The mass was excised, and the neonate subsequently remained asymptomatic. This is the first reported case of necrotizing enterocolitis in the setting of a sacrococcygeal teratoma in a neonate. This case also underscores the importance of vigilant monitoring of neonates with sacrococcygeal teratoma for complications arising from its mass effect apart from routine hemodynamic monitoring.
一名在产前检查时发现尾骨区域有肿块的新生儿,在出生后第4天突然出现腹部情况恶化,伴有腹胀和血性抽出液。腹部X线片显示肠壁积气(坏死性小肠结肠炎IIa期),需要停止喂养并开始静脉使用抗生素。对肿块及腹部进行的计算机断层扫描显示,尾骨肿块向腹腔内延伸,推移肠袢,可能为II型骶尾部畸胎瘤。鉴于病变体积大且血管丰富,我们推测慢性肠管受压伴盗血可能导致了肠道缺血、淤滞以及随后的坏死性小肠结肠炎。肿块被切除,该新生儿随后未再出现症状。这是首例报道的新生儿骶尾部畸胎瘤合并坏死性小肠结肠炎的病例。该病例还强调了,除常规血流动力学监测外,对患有骶尾部畸胎瘤的新生儿进行密切监测以发现其肿块效应引起的并发症的重要性。