Iba K, Morii H, Wada M, Yasumoto R, Kishimoto T, Mitsuhashi T, Hojo K, Okahara T
Endocrinol Jpn. 1981 Oct;28(5):595-604. doi: 10.1507/endocrj1954.28.595.
A 24-yr-old male patient that suffered from chronic tetany since school age. At the age of 20 tetanic convulsions occurred due to hypocalcemia. His mother also had chronic tetany due to pseudohypoparathyroidism. At the age of 24, hypocalcemia caused by pseudohypoparathyroidism was noted. Hypopotassemia persisted even when the hypocalcemia improved with the administration of 1 alpha-hydroxycholecalciferol and calcium lactate. Other findings were normal blood pressure, high levels of plasma renin activity and serum aldosterone, a fall in blood pressure after angiotensin II antagonist infusion, blunted pressor response to angiotensin II infusion and hyperplasia of the juxtaglomerular cells. These results were compatible with Bartter's syndrome. Plasma prostaglandins E2 and F2 alpha in standing position were suppressed after indomethacin administration. To our knowledge this is thought to be the first report of a case of pseudohypoparathyroidism associated with probable Bartter's syndrome.
一名24岁男性患者自学龄期起就患有慢性手足搐搦症。20岁时因低钙血症发生手足搐搦性惊厥。他的母亲也因假性甲状旁腺功能减退症患有慢性手足搐搦症。24岁时,发现由假性甲状旁腺功能减退症引起的低钙血症。即使在使用1α-羟胆钙化醇和乳酸钙使低钙血症改善后,低钾血症仍持续存在。其他检查结果为血压正常、血浆肾素活性和血清醛固酮水平升高、输注血管紧张素II拮抗剂后血压下降、对输注血管紧张素II的升压反应减弱以及肾小球旁细胞增生。这些结果符合巴特综合征。服用消炎痛后,站立位时血浆前列腺素E2和F2α受到抑制。据我们所知,这被认为是第一例与可能的巴特综合征相关的假性甲状旁腺功能减退症病例报告。