Kasuya H, Shimizu T, Nakamura S, Takakura K
Section of Neurosurgery, Saitamaken Saiseikai Kurihashi Hospital, Saitama, Japan.
Childs Nerv Syst. 1998 Jun;14(6):230-5. doi: 10.1007/s003810050218.
We report a 22-year-old man with hydrocephalus caused by aqueductal stenosis. The patient was diagnosed with Kabuki make-up syndrome based on associated findings such as a peculiar facies, postnatal growth deficiency, brachydactyly of the fifth fingers, undescended testes, and malrotation of the colon. Kabuki make-up syndrome, recognized in Japan in 1981, is characterized by five cardinal manifestations: a peculiar facies, skeletal anomalies, dermatoglyphic anomalies, slight to moderate mental retardation, and postnatal dwarfism. Neurological anomalies have been reported to include neonatal hypotonia, feeding problems, seizures, West syndrome, microcephaly, brain atrophy, GH deficiency, precocious puberty, delayed sexual development, and diabetes insipidus. Aqueductal stenosis may be caused by part of the series of midline anomalies. Physicians should pay attention to associated anomalous characteristics suggesting a malformation syndrome when they encounter nontumoral aqueductal stenosis in adolescents or adults.
我们报告一名22岁因导水管狭窄导致脑积水的男性患者。该患者根据特殊面容、出生后生长发育迟缓、第五指短指畸形、隐睾及结肠旋转不良等相关表现被诊断为歌舞伎综合征。歌舞伎综合征于1981年在日本被发现,其特征为五大主要表现:特殊面容、骨骼异常、皮纹异常、轻度至中度智力发育迟缓及出生后身材矮小。据报道,神经学异常包括新生儿肌张力减退、喂养问题、癫痫发作、韦斯特综合征、小头畸形、脑萎缩、生长激素缺乏、性早熟、性发育延迟及尿崩症。导水管狭窄可能是中线异常系列的一部分。当医生在青少年或成人中遇到非肿瘤性导水管狭窄时,应注意提示畸形综合征的相关异常特征。