Cajaiba Mariana M, Chojniak Martha M, Cunha Isabela W
Department of Anatomic Pathology, Hospital do Câncer AC Camargo-São Paulo, Brazil.
Pediatr Dev Pathol. 2008 Nov-Dec;11(6):479-81. doi: 10.2350/07-02-0231.1. Epub 2007 Jun 27.
Primary uveal-tract neoplasms are extremely rare in childhood; the most common lesions found are melanocytic. We report here the case of a 7-year-old girl who underwent enucleation of the right eye with clinical suspicion of choroid melanoma as a result of a ciliary body mass that extended to the posterior chamber. Histologically, the neoplasm featured spindle cell morphology, atypia, and mitoses. The tumor expressed smooth muscle alpha actin, pan-actin HHF-35, and desmin, whereas immunohistochemistry for melanocytic markers, such as S-100, Melan-A, and HMB-45, was negative. Based on these features, the diagnosis of leiomyosarcoma of the ciliary body was firmly established. Although several leiomyomas have been reported in the literature, there are only 2 previously reported cases of primary leiomyosarcoma of the uveal tract. Immunohistochemical expression of muscle proteins allowed distinction from the most common melanocytic tumors arising in this location.
原发性葡萄膜肿瘤在儿童时期极为罕见;最常见的病变是黑素细胞性的。我们在此报告一例7岁女孩的病例,该女孩因睫状体肿物延伸至后房,临床怀疑脉络膜黑色素瘤而接受了右眼眼球摘除术。组织学上,肿瘤具有梭形细胞形态、异型性和有丝分裂。肿瘤表达平滑肌α肌动蛋白、泛肌动蛋白HHF-35和结蛋白,而黑素细胞标志物如S-100、Melan-A和HMB-45的免疫组化结果为阴性。基于这些特征,确诊为睫状体平滑肌肉瘤。尽管文献中已报道了几例平滑肌瘤,但此前仅有2例原发性葡萄膜平滑肌肉瘤的报道。肌肉蛋白的免疫组化表达有助于将其与该部位最常见的黑素细胞肿瘤相鉴别。