IRCCS Fondazione Santa Lucia, Via del Fosso di Fiorano 64, 00143 Rome, Italy.
Neuroscience. 2012 Jun 1;211:165-84. doi: 10.1016/j.neuroscience.2011.06.075. Epub 2011 Jul 1.
Mutant huntingtin (mhtt) causes loss of synaptic plasticity and selective degeneration of striatal medium spiny neurons (MSNs), a core pathological feature of Huntington's disease (HD). However, projecting neurons become dysfunctional in the very early stages, long before death and this dysfunctional state may contribute to disease. Interneurons appear to be more resistant to the effects of mhtt and play important roles in supporting the activity of projecting neurons. Therefore, early modifications in the plasticity or in the pattern of cortical and striatal interneuronal activity may also be a factor in the alteration of the corticostriatal pathway in HD. While new models of HD provide information on the onset of complex behavioral changes, the mechanisms underlying alterations of the striatal microcircuit and their role in HD pathogenesis are still unclear. As a consequence, despite the development of new compounds, no adequate treatment is so far available to stop or reverse HD. Electrophysiological studies provide crucial information on neuronal dysfunction and circuit changes that underlie or precede symptoms. Here we review recent papers in which HD models have been used to study various aspects of neuronal physiology of corticostriatal pathway. We will also discuss advantages and limitations of rodent models compared to primate models and current challenges of therapies aimed at rescuing striatal function in HD.
突变亨廷顿蛋白(mhtt)导致突触可塑性丧失和纹状体中型棘突神经元(MSNs)选择性退化,这是亨廷顿病(HD)的核心病理学特征。然而,投射神经元在疾病发生之前的早期就出现了功能障碍,这种功能障碍状态可能会导致疾病的发生。中间神经元似乎对 mhtt 的影响具有更强的抵抗力,并在支持投射神经元的活动方面发挥着重要作用。因此,皮质和纹状体中间神经元活动的可塑性或模式的早期改变也可能是 HD 中皮质纹状体通路改变的一个因素。虽然新的 HD 模型提供了关于复杂行为变化开始的信息,但纹状体微电路改变的机制及其在 HD 发病机制中的作用仍不清楚。因此,尽管开发了新的化合物,但迄今为止,尚无有效的治疗方法可以阻止或逆转 HD。电生理研究提供了关于神经元功能障碍和导致或先于症状的电路变化的关键信息。在这里,我们回顾了最近的一些论文,这些论文使用 HD 模型研究了皮质纹状体通路的各种神经元生理学方面。我们还将讨论与灵长类模型相比,啮齿动物模型的优缺点,以及旨在挽救 HD 中纹状体功能的治疗方法目前面临的挑战。