Mariotti Cesare, Giovannini Alfonso, Reibaldi Michele, Nicolai Michele, Saitta Andrea
Ophthalmology Department, Polytechnic University of Marche, Ancona, Italy.
Department of Ophthalmology, University of Catania, Catania, Italy.
Case Rep Ophthalmol. 2014 May 29;5(2):162-7. doi: 10.1159/000363564. eCollection 2014 May.
A rare case of juxtapapillary retinal capillary hemangioma (JRCH) with tractional macular detachment that was managed successfully with minimally invasive 25-gauge vitreoretinal surgery, followed by two sessions of half-fluence photodynamic treatment (PDT) with good visual outcome, is presented. A 13-year-old female patient had progressive deterioration of the vision of her right eye due to the presence of tractional macular detachment associated with JRCH in von Hippel-Lindau (VHL) disease. A 25-gauge sutureless vitreoretinal surgery was successfully performed. Two months following surgery, the JRCH was treated with two sessions of half-fluence PDT at an interval of 4 months. Visual acuity improved from a preoperative level of 20/50 to 20/25 24 months postoperatively. Resolution of the tractional macular detachment, reduction of papillomacular area fluid, and reduction in size of the JRCH were observed during the follow-up period. No serious adverse events were observed. Small-gauge vitreoretinal surgery followed by PDT can be effective and safe in relieving tractional macular detachment and recovering useful visual acuity in JRCH in VHL disease.
本文报告了一例罕见的伴有牵拉性黄斑脱离的视乳头旁视网膜毛细血管瘤(JRCH),通过微创25G玻璃体视网膜手术成功治疗,随后进行了两次半量光动力治疗(PDT),视力恢复良好。一名13岁女性患者因患有与希佩尔-林道(VHL)病相关的JRCH并伴有牵拉性黄斑脱离,右眼视力逐渐下降。成功实施了25G无缝线玻璃体视网膜手术。术后两个月,对JRCH进行了两次半量PDT治疗,间隔4个月。术后24个月,视力从术前的20/50提高到了20/25。随访期间观察到牵拉性黄斑脱离消退、视乳头黄斑区积液减少以及JRCH大小缩小。未观察到严重不良事件。小切口玻璃体视网膜手术联合PDT对于缓解VHL病中JRCH所致的牵拉性黄斑脱离并恢复有用视力是有效且安全的。