Ameratunga Rohan, Barker Russell William, Steele Richard Henderson, Deo Maneka, Woon See-Tarn, Yeong Mee Ling, Koopmans Wikke
Department of Clinical Immunology, Auckland Hospital, Park Rd, Grafton, Auckland, 1010, New Zealand.
Department of Virology and Immunology, Auckland Hospital, Park Rd, Grafton, Auckland, 1010, New Zealand.
J Clin Immunol. 2015 Aug;35(6):589-94. doi: 10.1007/s10875-015-0189-6. Epub 2015 Aug 29.
When patients with hypogammaglobulinemia are encountered, a vigorous search should be undertaken for secondary treatable causes. Here we describe the first case of a patient with severe asymptomatic hypogammaglobulinemia where the underlying cause was undiagnosed celiac disease. A strict gluten free diet resulted in resolution of her mild long-standing abdominal symptoms and correction of her hypogammaglobulinemia. There was corresponding improvement in her duodenal histology and normalisation of her celiac serology. Protein losing enteropathy was unlikely to have been the mechanism of her profound hypogammaglobulinemia, as her albumin was within the normal range and she had a normal fecal alpha 1 antitrypsin level. Application of the Ameratunga et al. (2013) diagnostic criteria was helpful in confirming this patient did not have Common Variable Immunodeficiency Disorder (CVID). Celiac disease must now be considered in the differential diagnosis of severe hypogammaglobulinemia. There should be a low threshold for undertaking celiac serology in patients with hypogammaglobulinemia, even if they have minimal symptoms attributable to gut disease.
当遇到低丙种球蛋白血症患者时,应积极寻找可治疗的继发原因。在此,我们描述了首例严重无症状性低丙种球蛋白血症患者,其潜在病因是未确诊的乳糜泻。严格的无麸质饮食使她长期存在的轻度腹部症状得到缓解,低丙种球蛋白血症也得以纠正。她的十二指肠组织学相应改善,乳糜泻血清学指标恢复正常。蛋白丢失性肠病不太可能是其严重低丙种球蛋白血症的机制,因为她的白蛋白在正常范围内,且粪便α1抗胰蛋白酶水平正常。应用阿梅拉图加等人(2013年)的诊断标准有助于确认该患者没有常见变异型免疫缺陷病(CVID)。现在,乳糜泻必须被纳入严重低丙种球蛋白血症的鉴别诊断中。对于低丙种球蛋白血症患者,即使他们仅有轻微的肠道疾病相关症状,进行乳糜泻血清学检查的阈值也应较低。