Hameed Fawad, Steer Henry
Department of Respiratory Medicine, Musgrove Park Hospital, Taunton and Somerset NHS Foundation Trust, Taunton, UK.
Department of Respiratory Medicine, Gloucestershire Royal Hospital, Gloucestershire Hospitals NHS Foundation Trust, Gloucester, UK.
BMJ Case Rep. 2017 Aug 1;2017:bcr-2017-219822. doi: 10.1136/bcr-2017-219822.
A 57-year-old woman with SAPHO (synovitis-acne-pustulosis-hyperostosis-osteitis) syndrome presented with recurrent episodes of pneumonia. She was treated with multiple courses of antibiotics with no success. The transbronchial biopsy undertaken via bronchoscopy revealed organising pneumonia (OP). She was treated with steroids and responded well with full clinical recovery and normalisation of her chest X-ray.To our knowledge, this is the first reported case of OP in association with SAPHO syndrome. This case report highlights the importance of considering OP in patients with SAPHO syndrome who present with chest infection.
一名患有滑膜炎-痤疮-脓疱病-骨肥厚-骨炎(SAPHO)综合征的57岁女性反复出现肺炎发作。她接受了多疗程抗生素治疗但无效。通过支气管镜进行的经支气管活检显示为机化性肺炎(OP)。她接受了类固醇治疗,临床完全康复,胸部X线恢复正常,反应良好。据我们所知,这是首例报道的与SAPHO综合征相关的OP病例。本病例报告强调了在出现胸部感染的SAPHO综合征患者中考虑OP的重要性。