Suppr超能文献

1例闭塞性细支气管炎伴机化性肺炎合并SAPHO(滑膜炎-痤疮-脓疱病-骨肥厚-骨炎)综合征。

A case of bronchiolitis obliterans organising pneumonia associated with SAPHO (synovitis-acne-pustulosis-hyperostosis-osteitis) syndrome.

作者信息

Hameed Fawad, Steer Henry

机构信息

Department of Respiratory Medicine, Musgrove Park Hospital, Taunton and Somerset NHS Foundation Trust, Taunton, UK.

Department of Respiratory Medicine, Gloucestershire Royal Hospital, Gloucestershire Hospitals NHS Foundation Trust, Gloucester, UK.

出版信息

BMJ Case Rep. 2017 Aug 1;2017:bcr-2017-219822. doi: 10.1136/bcr-2017-219822.

Abstract

A 57-year-old woman with SAPHO (synovitis-acne-pustulosis-hyperostosis-osteitis) syndrome presented with recurrent episodes of pneumonia. She was treated with multiple courses of antibiotics with no success. The transbronchial biopsy undertaken via bronchoscopy revealed organising pneumonia (OP). She was treated with steroids and responded well with full clinical recovery and normalisation of her chest X-ray.To our knowledge, this is the first reported case of OP in association with SAPHO syndrome. This case report highlights the importance of considering OP in patients with SAPHO syndrome who present with chest infection.

摘要

一名患有滑膜炎-痤疮-脓疱病-骨肥厚-骨炎(SAPHO)综合征的57岁女性反复出现肺炎发作。她接受了多疗程抗生素治疗但无效。通过支气管镜进行的经支气管活检显示为机化性肺炎(OP)。她接受了类固醇治疗,临床完全康复,胸部X线恢复正常,反应良好。据我们所知,这是首例报道的与SAPHO综合征相关的OP病例。本病例报告强调了在出现胸部感染的SAPHO综合征患者中考虑OP的重要性。

相似文献

2
Synovitis-acne-pustulosis-hyperostosis-osteitis (SAPHO) Syndrome with Significant Bilateral Pleural Effusions.
Intern Med. 2017 Oct 15;56(20):2779-2783. doi: 10.2169/internalmedicine.8250-16. Epub 2017 Sep 15.
5
Synovitis, acne, pustulosis, hyperostosis, osteitis syndrome with invisible organizing pneumonia: A case report.
Int J Rheum Dis. 2023 Aug;26(8):1586-1589. doi: 10.1111/1756-185X.14631. Epub 2023 Feb 28.
10
Synovitis-acne-pustulosis-hyperostosis-osteitis Syndrome with Bilateral Pleural Effusion.
Intern Med. 2022 Sep 1;61(17):2671-2675. doi: 10.2169/internalmedicine.8473-21. Epub 2022 Feb 8.

引用本文的文献

1

本文引用的文献

1
Increased neutrophil infiltration, IL-1 production and a SAPHO syndrome-like phenotype in PSTPIP2-deficient mice.
Rheumatology (Oxford). 2015 Jul;54(7):1317-26. doi: 10.1093/rheumatology/keu481. Epub 2015 Jan 18.
3
SAPHO syndrome--a pictorial assay.
Iowa Orthop J. 2012;32:189-95.
5
Characterization of the immune response in the synovitis, acne, pustulosis, hyperostosis, osteitis (SAPHO) syndrome.
Rheumatology (Oxford). 2008 Aug;47(8):1160-7. doi: 10.1093/rheumatology/ken185. Epub 2008 Jun 17.
6
Is SAPHO syndrome a target for antibiotic therapy?
Clin Rheumatol. 2007 May;26(5):817-20. doi: 10.1007/s10067-006-0274-6. Epub 2006 Apr 7.
7
[SAPHO syndrome].
Rev Prat. 2004 Oct 15;54(15):1635-6.
10
Increased expression of the interleukin-10 gene by alveolar macrophages in interstitial lung disease.
Am J Physiol. 1997 Sep;273(3 Pt 1):L676-83. doi: 10.1152/ajplung.1997.273.3.L676.

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验