Sorrenti Giovanni, Pelligra Irene, Albertini Riccardo, Piccin Ottavio
Department of Otolaryngology Head and Neck Surgery, S. Orsola, Malpighi University Hospital, Via Massarenti 9, 40138 Bologna, Italy.
J Maxillofac Oral Surg. 2018 Dec;17(4):441-443. doi: 10.1007/s12663-017-1053-4. Epub 2017 Nov 9.
Solitary fibrous tumor is an uncommon mesenchymal neoplasm that may be found in any location. To date, only a few cases of solitary fibrous tumor involving the tongue have been reported.
We present the case of a 31-year-old man with a history of progressively worsening snoring and daytime sleepiness. Polysomnography revealed severe obstructive sleep apnea. An attempt to treat sleep apnea by continuous positive airway pressure and oral appliance led to a poor clinical response. CT and MRI scans findings revealed a large mass in the tongue base partially obstructing the airway. After the excision of the mass all symptoms, included daytime somnolence, disappeared and a polysomnographic examination showed the normalization of the somnographic parameters.
Although OSA is rarely caused by tumors, each patient with sleep disorders breathing should be examined carefully for the potential presence of an upper aero-digestive tract neoplasm that may contribute to obstruction.
孤立性纤维瘤是一种罕见的间叶性肿瘤,可发生于任何部位。迄今为止,仅有少数累及舌部的孤立性纤维瘤病例报道。
我们报告一例31岁男性患者,有打鼾及日间嗜睡进行性加重病史。多导睡眠图显示严重阻塞性睡眠呼吸暂停。尝试通过持续气道正压通气及口腔矫治器治疗睡眠呼吸暂停,临床效果不佳。CT和MRI扫描结果显示舌根有一巨大肿块,部分阻塞气道。肿块切除后,所有症状包括日间嗜睡均消失,多导睡眠图检查显示睡眠图参数恢复正常。
尽管阻塞性睡眠呼吸暂停很少由肿瘤引起,但每例睡眠呼吸障碍患者均应仔细检查,以排查可能导致阻塞的上呼吸道消化道肿瘤。