Mechineni Ashesha, Singh Balraj, Manickam Rajapriya
Internal Medicine, St. Joseph's University Medical Center, Paterson, USA.
Hematology/Oncology, St. Joseph's University Medical Center, Paterson, USA.
Cureus. 2021 Feb 15;13(2):e13347. doi: 10.7759/cureus.13347.
Swyer-James-Macleod syndrome (SJMS) is a rare clinical entity acquired during childhood due to a respiratory infection leading to bronchiolitis obliterans. This inciting event is hypothesized to cause structural and functional changes of the developing alveoli, terminal bronchioles, and the corresponding pulmonary vasculature, resulting in emphysematous changes and a matched ventilation-perfusion defect. We present a 67-year-old male patient with hypercapnic respiratory failure requiring invasive mechanical ventilation, who had typical features of SJMS undiagnosed before this admission. He was extubated successfully, discharged home, and continues to be stable at a 90-day follow-up period. This marks one of the rare accounts where a patient with SJMS was given ventilatory support emergently, and one of the oldest patients reported. SJMS is under-reported due to its indolent clinical course and misdiagnosed as some other pulmonary abnormality. The clinical course progression and prognosis are unclear and variable in many affected patients due to this condition's rarity.
斯怀尔-詹姆斯-麦克劳德综合征(SJMS)是一种儿童期获得性罕见临床病症,由导致闭塞性细支气管炎的呼吸道感染引起。据推测,这一诱发事件会导致发育中的肺泡、终末细支气管以及相应肺血管发生结构和功能改变,从而导致肺气肿改变以及匹配的通气-灌注缺陷。我们报告一名67岁男性患者,因高碳酸血症性呼吸衰竭需要有创机械通气,该患者具有SJMS的典型特征,此次入院前未被诊断出来。他成功拔管,出院回家,在90天的随访期内持续保持稳定。这是罕见的为SJMS患者紧急给予通气支持的病例之一,也是所报道的年龄最大的患者之一。由于SJMS临床病程隐匿且常被误诊为其他肺部异常,因此报告不足。由于这种病症罕见,许多受影响患者的临床病程进展和预后尚不清楚且存在差异。