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小儿筛窦浆液黏液性错构瘤(病例报告)

Seromucinous hamartoma of ethmoid sinus in pediatric patient (case report).

作者信息

Alokby Ghassan, Alayed Rawan S, Al Fayez Jude B

机构信息

King Faisal Specialist Hospital and Research Center in Riyadh, Al Faisal University, Al mathar Ash shamali, 11564 Riyadh, Saudi Arabia; Clinical fellowship in Rhinology and Paranasal Sinus Surgery at the University of Iowa Hospital and Clinics, Iowa City, IA, USA; Clinical fellowship in Rhinology and Endoscopic Skull Base Surgery at the University of Miami Miller School of Medicine, Miami, FL, USA.

King Faisal Specialist Hospital and Research Center in Riyadh, Al Faisal University, Al mathar Ash shamali, 11564 Riyadh, Saudi Arabia; Saudi Board in Otolaryngology- Head and Neck Surgery, 14215 Riyadh, Saudi Arabia.

出版信息

Int J Surg Case Rep. 2021 May;82:105915. doi: 10.1016/j.ijscr.2021.105915. Epub 2021 Apr 27.

Abstract

INTRODUCTION AND IMPORTANCE

Seromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium, which was originally described by Baillie and Batsakis in 1974. Since this time, case reports started to be published on SH, as a middle aged and elderly disease, here we report a case of a pediatric patient who found to have SH.

PRESENTATION OF THE CASE

2-year-old girl, brought by her parent with a complain of a mass at the right medial canthal area for one year.

CLINICAL DISCUSSION

As this pediatric patient presented with long standing history of right medial canthal area, we made out differential diagnosis list, with keeping congenital midline nasal masses such as nasal glioma, dermoid, and encephalocele at the top of our differentials, followed by inflammatory disease and lacreimal system disease. After bedside clinical assessment and imaging, patient underwent endoscopic sinus surgery for surgical excision, histopathology analysis came as Seromucinous hamartoma. Postoperative course was unremarkable, patient is disease- free for 18 months, till her most recent follow up. With no additional treatment or recurrence.

CONCLUSION

This case report indicates that seromucinous hamartoma should always be considered in the differential diagnosis of pediatric sinonasal disease. According to the literature review we did; this is the first case reported in such an age group.

摘要

引言与重要性

浆液黏液性错构瘤是一种罕见的起源于呼吸道上皮的良性腺体增生,最初由贝利和巴塔基斯于1974年描述。从那时起,关于浆液黏液性错构瘤的病例报告开始发表,该病多见于中老年患者,在此我们报告一例患有浆液黏液性错构瘤的儿科患者。

病例介绍

一名2岁女孩,由其家长带来,主诉右侧内眦区有肿物1年。

临床讨论

由于该儿科患者有右侧内眦区长时间肿物的病史,我们列出了鉴别诊断清单,首先考虑先天性中线鼻部肿物,如鼻胶质瘤、皮样囊肿和脑膨出,其次是炎症性疾病和泪器系统疾病。经过床边临床评估和影像学检查后,患者接受了鼻内镜鼻窦手术以切除肿物,组织病理学分析显示为浆液黏液性错构瘤。术后病程平稳,患者在最近一次随访前已无病生存18个月,未进行额外治疗,也无复发。

结论

本病例报告表明,在儿科鼻窦疾病的鉴别诊断中应始终考虑浆液黏液性错构瘤。根据我们所做的文献综述,这是该年龄组报道的首例病例。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/2ad9/8113836/290c915ba613/gr1.jpg

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