Champion G D, Saxon J A, Kossard S
Department of Rheumatology, St. Vincent's Hospital, Sydney, Australia.
J Rheumatol. 1987 Dec;14(6):1196-8.
A 45-year-old woman developed simultaneously a form of palmar and digital fibromatosis and an unusual polyarticular disorder with painful capsular contraction. The features of the bilateral shoulder involvement were consistent with the adhesive capsulitis/frozen shoulder syndrome. The other affected joints were painfully contracted and tender but without signs of inflammation in synovial fluid (knee) or associated abnormalities in hematologic status. Histologically, there was extensive fibrosis with increased numbers of fibroblasts, dilated blood vessels and scant perivascular lymphocytic infiltration. The clinical and pathological features were similar to cases described as palmar fasciitis and polyarthritis occurring in association with malignant tumors and with antituberculous chemotherapy. Several months after removal of an endometrial cyst of the ovary and after symptomatic treatment, the palmar fibromatosis and polyarticular disorder had almost completely resolved.
一名45岁女性同时患上了一种掌部和指部纤维瘤病以及一种伴有疼痛性关节囊挛缩的不寻常多关节疾病。双侧肩部受累的特征符合粘连性关节囊炎/肩周炎综合征。其他受累关节出现疼痛性挛缩且有压痛，但滑膜液（膝关节）无炎症迹象，血液学状态也无相关异常。组织学检查显示，存在广泛纤维化，成纤维细胞数量增加，血管扩张，血管周围有少量淋巴细胞浸润。临床和病理特征与描述为与恶性肿瘤及抗结核化疗相关的掌腱膜挛缩症和多关节炎的病例相似。在切除卵巢的子宫内膜囊肿并进行对症治疗几个月后，掌部纤维瘤病和多关节疾病几乎完全缓解。
