Department of Physiology and Biophysics, University of Illinois at Chicago, Chicago, Illinois, USA.
Department of Biomedical Engineering, University of Illinois at Chicago, Chicago, Illinois, USA.
Physiol Rep. 2022 Mar;10(5):e15207. doi: 10.14814/phy2.15207.
Age-related wild-type transthyretin amyloidosis (wtATTR) is characterized by systemic deposition of amyloidogenic fibrils of misfolded transthyretin (TTR) in the connective tissue of many organs. In the heart, this leads to age-related heart failure with preserved ejection fraction (HFpEF). The hypothesis tested is that TTR deposited in vitro disrupts cardiac myocyte cell-to-cell and cell-to-matrix adhesion complexes, resulting in altered calcium handling, force generation, and sarcomeric disorganization. Human iPSC-derived cardiomyocytes and neonatal rat ventricular myocytes (NRVMs), when grown on TTR-coated polymeric substrata mimicking the stiffness of the healthy human myocardium (10 kPa), had decreased contraction and relaxation velocities as well as decreased force production measured using traction force microscopy. Both NRVMs and adult mouse atrial cardiomyocytes had altered calcium kinetics with prolonged transients when cultured on TTR fibril-coated substrates. Furthermore, NRVMs grown on stiff (~GPa), flat or microgrooved substrates coated with TTR fibrils exhibited significantly decreased intercellular electrical coupling as shown by FRAP dynamics of cells loaded with the gap junction-permeable dye calcein-AM, along with decreased gap junction content as determined by quantitative connexin 43 staining. Significant sarcomeric disorganization and loss of sarcomere content, with increased ubiquitin localization to the sarcomere, were seen in NRVMs on various TTR fibril-coated substrata. TTR presence decreased intercellular mechanical junctions as evidenced by quantitative immunofluorescence staining of N-cadherin and vinculin. Current therapies for wtATTR are cost-prohibitive and only slow the disease progression; therefore, better understanding of cardiomyocyte maladaptation induced by TTR amyloid may identify novel therapeutic targets.
年龄相关性野生型转甲状腺素蛋白淀粉样变性(wtATTR)的特征是在许多器官的结缔组织中,错误折叠的转甲状腺素蛋白(TTR)的淀粉样纤维全身沉积。在心脏中,这会导致与年龄相关的射血分数保留型心力衰竭(HFpEF)。该研究检验的假设是,体外沉积的 TTR 破坏了心肌细胞细胞间和细胞与基质黏附复合物,导致钙处理、力生成和肌节结构紊乱改变。当在模拟健康人心肌组织刚度(10kPa)的 TTR 涂层聚合物基质上培养人诱导多能干细胞(iPSC)衍生的心肌细胞和新生大鼠心室肌细胞(NRVM)时,收缩和舒张速度以及使用牵引力显微镜测量的力产生都会降低。当在 TTR 纤维涂层底物上培养时,NRVM 和成年小鼠心房肌细胞的钙动力学都会发生改变,瞬时延长。此外,在 TTR 纤维涂层的刚性(~GPa)、平坦或微槽基底上生长的 NRVM 表现出明显降低的细胞间电偶联,通过用间隙连接通透染料 calcein-AM 负载的细胞 FRAP 动力学显示,以及通过定量连接蛋白 43 染色确定的间隙连接含量降低。在各种 TTR 纤维涂层基质上的 NRVM 中观察到明显的肌节结构紊乱和肌节含量减少,肌球蛋白重链定位到肌节增加。TTR 的存在减少了细胞间机械连接,这可以通过定量免疫荧光染色 N-钙黏蛋白和波形蛋白来证明。目前用于治疗 wtATTR 的疗法费用昂贵,并且只能减缓疾病进展;因此,更好地了解 TTR 淀粉样蛋白诱导的心肌细胞失调可能会确定新的治疗靶点。