Nadi Anass, Benhayoun Yassamin, Cherkaoui Reda, Delsa Hanane, Rouibaa Fedoua
Gastroenterology and Hepatology, Faculty of Medicine, Mohammed VI University of Health Sciences (UM6SS), Casablanca, MAR.
Gastroenterology, Faculty of Medicine, Mohammed VI University of Health Sciences (UM6SS), Casablanca, MAR.
Cureus. 2022 Jul 8;14(7):e26657. doi: 10.7759/cureus.26657. eCollection 2022 Jul.
IgG4-related disease (IgG4-RD) is an emerging immune-mediated disease that can involve any organ. The involvement of the pancreas and biliary tract is the most common and well-studied in the literature. It is characterized by a non-specific presentation, mimicking a malignant process. The goal was to look at the different clinical and paraclinical aspects of this disease, as well as the challenges that come from its management. It was made up of three observations of patients with IgG4-RD involving the biliary tract and pancreas. The first observation concerned intrahepatic biliary cholangitis that was accompanied by porto-mesenteric thrombosis, which was discovered by cholestatic jaundice on the 15th day after an appendectomy, and the patient improved under corticosteroids and anticoagulants. The second observation concerned an acute revelation of the disease. It was an acute attack of chronic pancreatitis of IgG4-RD. The main symptoms were pancreatic pain and exocrine pancreatic insufficiency, and corticosteroid therapy allowed remission. The third observation was related to autoimmune pancreatitis (AIP) and IgG4-related sclerosing cholangitis, revealed by jaundice with cholestasis. The patient acquired corticosteroid resistance and an adverse progression to decompensated cirrhosis, and liver transplantation was indicated. The clinical presentation of IgG4-RD is heterogeneous, as evidenced by our three clinical observations. There are still significant gaps in our understanding, particularly in terms of pathogenesis and factors that influence therapy response. Further observational and interventional research is needed to better manage this disease.
IgG4相关性疾病(IgG4-RD)是一种新出现的免疫介导性疾病,可累及任何器官。胰腺和胆道受累最为常见,也是文献中研究最多的。其特征为表现不特异,类似恶性病变。目的是研究该疾病不同的临床和辅助检查方面,以及其治疗中面临的挑战。研究由3例IgG4-RD累及胆道和胰腺的患者病例组成。第一例病例为肝内胆管炎伴门静脉肠系膜血栓形成,在阑尾切除术后第15天因胆汁淤积性黄疸发现,患者在使用糖皮质激素和抗凝剂治疗后病情好转。第二例病例为疾病急性起病,是IgG4-RD慢性胰腺炎的急性发作,主要症状为胰腺疼痛和胰腺外分泌功能不全,糖皮质激素治疗后病情缓解。第三例病例与自身免疫性胰腺炎(AIP)和IgG4相关性硬化性胆管炎有关,因胆汁淤积性黄疸而发现,患者出现糖皮质激素抵抗且病情进展至失代偿期肝硬化,遂行肝移植。我们的3例临床病例证明,IgG4-RD的临床表现具有异质性。我们在认识上仍存在重大差距,尤其是在发病机制和影响治疗反应的因素方面。需要进一步开展观察性和干预性研究,以更好地治疗该疾病。