Charlaix Hidalgo Ana Lucia, Roux Alexia, Charissoux Aurelie, Mathonnet Muriel, Descazeaud Aurelien, Durand Fontanier Sylvaine, Taibi Abdelkader
Digestive Surgery Department, Dupuytren Limoges University Hospital, Limoges, France.
Pathology Department, Dupuytren Limoges University Hospital, Limoges, France.
Indian J Surg Oncol. 2023 Jun;14(Suppl 1):92-96. doi: 10.1007/s13193-022-01693-6. Epub 2023 Jan 4.
Multicystic benign mesothelioma is a rare tumor that affects the serosa. Most cases present with peritoneal lesions exclusively. Some identified risk factors are chronic abdominal inflammation, woman of childbearing age, and asbestos exposure. The symptomatology is not specific and can delay the diagnosis. There are no guidelines for the treatment of this pathology. We describe one male patient with abdominal and tunica vaginalis localizations of multicystic benign mesothelioma. The diagnosis was suspected on imaging and confirmed with histological examination. The treatment on an expert center was complete cytoreduction surgery and HIPEC, but the patient had two recurrences during the 2-year of follow-up. This is the first case of simultaneous rare localizations of multicystic benign mesothelioma. No new risk factors were identified. The case underlines the importance of regular examination of all serosa localizations.
多囊性良性间皮瘤是一种罕见的累及浆膜的肿瘤。大多数病例仅表现为腹膜病变。一些已确定的危险因素包括慢性腹部炎症、育龄期女性和石棉暴露。其症状不具有特异性,可能会延迟诊断。目前尚无针对这种病理情况的治疗指南。我们描述了一名患有多囊性良性间皮瘤腹部和鞘膜定位的男性患者。影像学检查怀疑诊断,并经组织学检查确诊。在专家中心进行的治疗是完全细胞减灭术和腹腔热灌注化疗(HIPEC),但患者在2年的随访期间出现了两次复发。这是首例多囊性良性间皮瘤同时出现罕见定位的病例。未发现新的危险因素。该病例强调了对所有浆膜定位进行定期检查的重要性。