York Trials Unit, Department of Health Sciences, University of York, Heslington, York, YO10 5DD, UK.
Department of Statistical Sciences 'Paolo Fortunati', University of Bologna, Bologna, Italy.
BMC Med Res Methodol. 2024 Jul 19;24(1):155. doi: 10.1186/s12874-024-02248-9.
There is increasing interest in the capacity of adaptive designs to improve the efficiency of clinical trials. However, relatively little work has investigated how economic considerations - including the costs of the trial - might inform the design and conduct of adaptive clinical trials.
We apply a recently published Bayesian model of a value-based sequential clinical trial to data from the 'Hydroxychloroquine Effectiveness in Reducing symptoms of hand Osteoarthritis' (HERO) trial. Using parameters estimated from the trial data, including the cost of running the trial, and using multiple imputation to estimate the accumulating cost-effectiveness signal in the presence of missing data, we assess when the trial would have stopped had the value-based model been used. We used re-sampling methods to compare the design's operating characteristics with those of a conventional fixed length design.
In contrast to the findings of the only other published retrospective application of this model, the equivocal nature of the cost-effectiveness signal from the HERO trial means that the design would have stopped the trial close to, or at, its maximum planned sample size, with limited additional value delivered via savings in research expenditure.
Evidence from the two retrospective applications of this design suggests that, when the cost-effectiveness signal in a clinical trial is unambiguous, the Bayesian value-adaptive design can stop the trial before it reaches its maximum sample size, potentially saving research costs when compared with the alternative fixed sample size design. However, when the cost-effectiveness signal is equivocal, the design is expected to run to, or close to, the maximum sample size and deliver limited savings in research costs.
适应性设计提高临床试验效率的能力越来越受到关注。然而,相对较少的工作调查了经济考虑因素(包括试验成本)如何为适应性临床试验的设计和实施提供信息。
我们将最近发表的基于价值的序贯临床试验贝叶斯模型应用于“羟氯喹在手骨关节炎症状减轻中的有效性”(HERO)试验的数据。使用从试验数据估计的参数,包括运行试验的成本,并使用多重插补来估计在存在缺失数据的情况下累积的成本效益信号,我们评估了如果使用基于价值的模型,试验何时会停止。我们使用重新抽样方法比较了设计的操作特性与传统固定长度设计的操作特性。
与该模型唯一的另一次回溯应用的结果相反,HERO 试验的成本效益信号的不确定性意味着设计将接近或达到其最大计划样本量停止试验,通过节省研究支出提供有限的额外价值。
这两个设计回溯应用的证据表明,当临床试验中的成本效益信号明确时,贝叶斯价值自适应设计可以在达到最大样本量之前停止试验,与替代的固定样本量设计相比,可能节省研究成本。然而,当成本效益信号不确定时,预计设计将达到或接近最大样本量,并在研究成本方面节省有限的成本。