Dreborg S, Erikson A, Hagberg B
Eur J Pediatr. 1980 Mar;133(2):107-18. doi: 10.1007/BF00441578.
We report follow-up studies of 22 cases of the Norrbottnian type of Gaucher disease ("type III"). The series was divided into 2 main groups of families depending on their birth province (Norrbotten, Västerbotten). The distribution and types of organ manifestations and complications were the same in both groups, each of which was considered to be genotypically homogeneous. The severity of the clinical symptoms and signs and the course of the disease differed markedly not only between families but also between siblings. Splenectomy accelerated deterioration, particularly with regard to skeletal and central nervous system manifestations. On a clinical basis it is concluded that the Norrbottnian type of Gaucher disease, which has now been diagnosed in about 40 cases, is probably due to a unique mutation which may have happened several hundred of years ago in northern Sweden.
我们报告了22例诺尔伯特型戈谢病(“III型”)的随访研究。根据出生省份(诺尔伯特、西博滕),该系列分为2个主要的家族组。两组器官表现和并发症的分布及类型相同,每组在基因型上均被认为是同质的。临床症状和体征的严重程度以及疾病进程不仅在家族之间,而且在兄弟姐妹之间都有显著差异。脾切除术加速了病情恶化,尤其是在骨骼和中枢神经系统表现方面。基于临床得出结论,目前已诊断出约40例的诺尔伯特型戈谢病可能是由于数百年前在瑞典北部发生的一次独特突变所致。